U.O.C. Genetica Medica, IRCCS Istituto Giannina Gaslini, Genova, Italy.
Laboratorio Cellule Staminali Post Natali e Terapie Cellulari, IRCCS Istituto Giannina Gaslini, Genova, Italy.
PLoS One. 2020 Dec 16;15(12):e0244069. doi: 10.1371/journal.pone.0244069. eCollection 2020.
In a previous study, we demonstrated that CHL1, the neuronal cell adhesion molecule close homolog of L1, acts as a tumor suppressor in human neuroblastoma (NB), a still highly lethal childhood malignancy, influencing its differentiation and proliferation degree. Here we found that ezrin, one of the ERM (ezrin, radixin, moesin) proteins involved in cytoskeleton organization, strongly interacts with CHL1. The low expression of EZRIN, as well as the low expression of CHL1 and of the neuronal differentiation marker MAP2, correlates with poor outcome in NB patients. Knock-down of ezrin in HTLA-230 cell line induces neurite retraction, enhances cell proliferation and migration, and triggers anchorage-independent growth, with effects very similar to those already obtained by CHL1 silencing. Furthermore, lack of ezrin inhibits the expression of MAP2 and of the oncosuppressor molecule p53, whereas it enhances MAPK activation, all typical features of tumor aggressiveness. As already described, CHL1 overexpression in IMR-32 cell line provokes an opposite trend, but the co-silencing of ezrin reduces these effects, confirming the hypothesis that CHL1 acts in close connection with ezrin. Overall, our data show that ezrin reinforces the differentiating and oncosuppressive functions of CHL1, identifying this ERM protein as a new targetable molecule for NB therapy.
在之前的研究中,我们证明了神经元细胞黏附分子 CHL1 的同系物 L1 在人神经母细胞瘤(NB)中作为一种肿瘤抑制因子发挥作用,NB 是一种仍然具有高度致命性的儿童恶性肿瘤,影响其分化和增殖程度。在这里,我们发现参与细胞骨架组织的 ERM(ezrin、radixin、moesin)蛋白之一 ezrin 与 CHL1 强烈相互作用。EZRIN 的低表达以及 CHL1 和神经元分化标志物 MAP2 的低表达与 NB 患者的不良预后相关。在 HTLA-230 细胞系中敲低 ezrin 会诱导轴突回缩,增强细胞增殖和迁移,并引发非依赖性生长,其效果与 CHL1 沉默已获得的效果非常相似。此外,缺乏 ezrin 会抑制 MAP2 和抑癌分子 p53 的表达,而增强 MAPK 激活,这些都是肿瘤侵袭性的典型特征。正如已经描述的,CHL1 在 IMR-32 细胞系中的过表达会引起相反的趋势,但 ezrin 的共沉默会降低这些效果,证实了 CHL1 与 ezrin 密切相关的假设。总体而言,我们的数据表明,ezrin 增强了 CHL1 的分化和抑瘤功能,将这种 ERM 蛋白确定为 NB 治疗的新靶向分子。