Hattori Aiji, Hamada Yasuhiko, Kawabata Hiroyuki, Tanaka Kyosuke
Department of Gastroenterology Saiseikai Matsusaka General Hospital Matsusaka Japan.
Department of Gastroenterology and Hepatology Mie University Hospital Tsu Japan.
JGH Open. 2020 Oct 22;5(1):166-168. doi: 10.1002/jgh3.12439. eCollection 2021 Jan.
We present a 23-year-old man with hemophagocytic lymphohistiocytosis (HLH) triggered by Epstein-Bar virus (EBV) infection. This patient presented with persistent fever and acute liver injury 6 weeks after having an infectious mononucleosis associated with EBV infection. He had hypofibrinogenemia, hyperferritinemia, increased soluble interleukin-2 receptor, elevated prothrombin time, and pancytopenia. Bone marrow examination for evaluation of pancytopenia revealed that macrophages had phagocytosed mature erythrocytes. Based on these findings, we suspected an HLH triggered by EBV infection (EBV-HLH). To distinguish from HLH triggered by malignant lymphomas accompanying EBV infection, we performed a percutaneous liver biopsy, which revealed that atypical T-lymphocytes had infiltrated the liver tissues. The T-lymphocytes were positive for EBV-encoded RNA in situ hybridization, and no distinct monoclonal T-cell receptor chain gene rearrangement was detected. These findings indicated EBV hepatitis and, accordingly, malignant lymphoma was ruled out. We finally made a diagnosis of EBV-HLH. The patient was treated with corticosteroid and etoposide, according to HLH-2004 guideline recommendations, and the patient's symptoms and laboratory values improved. After that, he experienced no recurrence. Prompt recognition and initiation of treatment remains the key to the survival of patients with EBV-HLH, and the liver biopsy was helpful in making the diagnosis.
我们报告一名23岁男性,因感染爱泼斯坦-巴尔病毒(EBV)引发噬血细胞性淋巴组织细胞增生症(HLH)。该患者在患与EBV感染相关的传染性单核细胞增多症6周后,出现持续发热和急性肝损伤。他存在低纤维蛋白原血症、高铁蛋白血症、可溶性白细胞介素-2受体升高、凝血酶原时间延长及全血细胞减少。对全血细胞减少进行评估的骨髓检查显示,巨噬细胞吞噬了成熟红细胞。基于这些发现,我们怀疑是由EBV感染引发的HLH(EBV-HLH)。为了与EBV感染伴发的恶性淋巴瘤引发的HLH相鉴别,我们进行了经皮肝活检,结果显示非典型T淋巴细胞浸润了肝组织。原位杂交显示这些T淋巴细胞EBV编码的RNA呈阳性,未检测到明显的单克隆T细胞受体链基因重排。这些发现提示为EBV肝炎,因此排除了恶性淋巴瘤。我们最终诊断为EBV-HLH。根据HLH-2004指南建议,该患者接受了糖皮质激素和依托泊苷治疗,其症状和实验室检查值均有所改善。此后,他未再复发。及时识别并开始治疗仍然是EBV-HLH患者生存的关键,肝活检有助于做出诊断。