Department of Obstetrics and Gynaecology, Olabisi Onabanjo University Teaching Hospital, Olabisi Onabanjo University Sagamu, Ogun state, Nigeria.
Department of Radiology Olabisi Onabanjo University Sagamu, Sagamu, Nigeria.
Pan Afr Med J. 2020 Nov 5;37:220. doi: 10.11604/pamj.2020.37.220.21211. eCollection 2020.
A case of thanatophoric dysplasia with sudden death at term is hereby presented. Thanatophoric dysplasia is an uncommon, lethal skeletal dysplasia which is associated with mutation in the extracellular region of fibroblast growth factor receptor 3 (FGFR3). It is an autosommal dominant condition that has sporadic occurrence and early ultrasound scan has not been of great benefit in its detection. Diagnosis is mostly made in the third trimester. The fetal death is usually due to severe respiratory insufficiency from a reduced thoracic capacity and hypoplastic lungs and/or respiratory failure due to brainstem compression. In view of the autosomal dominance of TD, it will be advisable for a woman with previous history to have prenatal screening to relieve parental anxiety and prevent late detection.
现报告一例足月致死性致死性骨发育不良病例。致死性骨发育不良是一种罕见的致死性骨骼发育不良,与成纤维细胞生长因子受体 3(FGFR3)细胞外区的突变有关。它是一种常染色体显性疾病,具有散发性,早期超声扫描对其检测没有很大帮助。诊断大多在孕晚期进行。胎儿死亡通常是由于胸廓容量减少和肺发育不良导致严重呼吸功能不全,和/或由于脑干受压导致呼吸衰竭。鉴于 TD 的常染色体显性遗传,对于有既往病史的女性,进行产前筛查是明智的,可以减轻父母的焦虑并防止晚期发现。