Truong Thai, Nguyen Hang Thi Tuyet, Phan Vien Thi Xuan, Ly Minh Huong Phu, Phan Van Thi Tuong, Phan Tu Anh, Phan Hannah Hue, Tran Phillip
Department of Internal Medicine, University of Medicine and Pharmacy at Ho Chi Minh City, Vietnam.
Cho Ray Hospital, Ho Chi Minh City, Vietnam.
AME Case Rep. 2021 Jan 25;5:10. doi: 10.21037/acr-20-100. eCollection 2021.
Coronary pulmonary artery fistula (CPAF) is a rare entity in the population. It may present with multiple clinical settings and in various age ranges. Invasive coronary angiography (ICA), coronary computed tomography angiography (CCTA), and transthoracic echocardiography (TTE) have been reported as diagnostic tools for CPAF. Among them, TTE is rarely capable of identifying CPAF. There is no current treatment guideline as some of the interventional therapies are effective yet controversial. The therapy therefore should be individualized. We report a case of CPAF accidentally detected by TTE in a 93-year-old female who presented with acute respiratory distress on the setting of community-acquired pneumonia, diastolic heart failure, ischemic heart disease, pulmonary hypertension, chronic kidney disease, and hypertension. The patient presented with orthopnea, fever, bilateral pleuritic chest pain, and productive cough with yellowish sputum for 7 days. She had no previous chest trauma or surgical intervention. TTE demonstrated the tortuous enlargement of left coronary artery which drains into the pulmonary arterial trunk right above the pulmonary valve. As the patient was in advanced age with multiple comorbidities; we offered a conservative management including diuretic, oxygen therapy, antibiotic, antiplatelet, and statin. She recovered following a 13-day hospitalization. To our knowledge, this is the oldest case report of suspected congenital CPAF which is particularly detected by TTE.
冠状动脉肺动脉瘘(CPAF)在人群中是一种罕见的病症。它可能在多种临床情况下出现,且涉及不同年龄范围。有报道称,有创冠状动脉造影(ICA)、冠状动脉计算机断层扫描血管造影(CCTA)和经胸超声心动图(TTE)可作为CPAF的诊断工具。其中,TTE很少能够识别CPAF。由于一些介入治疗虽有效但存在争议,目前尚无治疗指南。因此,治疗应个体化。我们报告一例93岁女性患者,因社区获得性肺炎、舒张性心力衰竭、缺血性心脏病、肺动脉高压、慢性肾脏病和高血压而出现急性呼吸窘迫,TTE意外检测到其患有CPAF。患者出现端坐呼吸、发热、双侧胸膜炎性胸痛以及咳黄色脓性痰7天。她既往无胸部外伤或手术史。TTE显示左冠状动脉迂曲增粗,引流至肺动脉瓣上方的肺动脉干。鉴于患者年龄较大且合并多种疾病,我们采取了包括利尿剂、氧疗、抗生素、抗血小板药物和他汀类药物在内的保守治疗。住院13天后她康复了。据我们所知,这是疑似先天性CPAF且特别由TTE检测到的最年长病例报告。