Department of Oncologic Pathology, Dana-Farber Cancer Institute, Harvard Medical School, Boston, MA.
Department of Experimental Hematology, Institute of Hematology and Transfusion Medicine, Warsaw, Poland.
Blood. 2021 Apr 8;137(14):1905-1919. doi: 10.1182/blood.2020009088.
Chromosome 13q deletion [del(13q)], harboring the miR-15a/16-1 cluster, is one of the most common genetic alterations in mature B-cell malignancies, which originate from germinal center (GC) and post-GC B cells. Moreover, miR-15a/16 expression is frequently reduced in lymphoma and multiple myeloma (MM) cells without del(13q), suggesting important tumor-suppressor activity. However, the role of miR-15a/16-1 in B-cell activation and initiation of mature B-cell neoplasms remains to be determined. We show that conditional deletion of the miR-15a/16-1 cluster in murine GC B cells induces moderate but widespread molecular and functional changes including an increased number of GC B cells, percentage of dark zone B cells, and maturation into plasma cells. With time, this leads to development of mature B-cell neoplasms resembling human extramedullary plasmacytoma (EP) as well as follicular and diffuse large B-cell lymphomas. The indolent nature and lack of bone marrow involvement of EP in our murine model resembles human primary EP rather than MM that has progressed to extramedullary disease. We corroborate human primary EP having low levels of miR-15a/16 expression, with del(13q) being the most common genetic loss. Additionally, we show that, although the mutational profile of human EP is similar to MM, there are some exceptions such as the low frequency of hyperdiploidy in EP, which could account for different disease presentation. Taken together, our studies highlight the significant role of the miR-15a/16-1 cluster in the regulation of the GC reaction and its fundamental context-dependent tumor-suppression function in plasma cell and B-cell malignancies.
13 号染色体缺失[del(13q)],携带 miR-15a/16-1 簇,是成熟 B 细胞恶性肿瘤中最常见的遗传改变之一,起源于生发中心 (GC) 和 GC 后 B 细胞。此外,miR-15a/16 在没有 del(13q)的淋巴瘤和多发性骨髓瘤 (MM) 细胞中表达经常降低,提示其具有重要的肿瘤抑制活性。然而,miR-15a/16-1 在 B 细胞激活和成熟 B 细胞肿瘤发生中的作用仍有待确定。我们表明,在 GC B 细胞中条件性缺失 miR-15a/16-1 簇会引起中度但广泛的分子和功能变化,包括 GC B 细胞数量增加、暗区 B 细胞比例增加以及向浆细胞成熟。随着时间的推移,这会导致成熟 B 细胞肿瘤的发展,类似于人类骨髓外浆细胞瘤 (EP) 以及滤泡性和弥漫性大 B 细胞淋巴瘤。我们的小鼠模型中 EP 的惰性性质和缺乏骨髓受累类似于人类原发性 EP,而不是已经进展为骨髓外疾病的 MM。我们证实人类原发性 EP 的 miR-15a/16 表达水平较低,del(13q)是最常见的遗传缺失。此外,我们表明,尽管人类 EP 的突变谱与 MM 相似,但也存在一些例外,例如 EP 中高频二倍体的低频率,这可能导致不同的疾病表现。总之,我们的研究强调了 miR-15a/16-1 簇在调节 GC 反应及其在浆细胞和 B 细胞恶性肿瘤中的基本上下文依赖性肿瘤抑制功能中的重要作用。