Department of Diagnostic and Interventional Radiology, Osaka International Cancer Institute, Japan.
Department of Diagnostic Radiology, Osaka Medical College, Japan.
Intern Med. 2021 Sep 15;60(18):3047-3050. doi: 10.2169/internalmedicine.6309-20. Epub 2021 Apr 5.
A 60-year-old woman presented with multiple lung and bone metastases with unknown primary cancer. Chest CT images showed multiple pulmonary cysts, predominantly of the middle and lower lobes. She also had a history of pneumothorax. Four years after chemotherapy and radiation therapy, multiple hypervascular tumors eventually developed in the bilateral kidneys, suggesting the possibility of Birt-Hogg-Dubé (BHD) syndrome. Genetic testing revealed a folliculin mutation, which confirmed the diagnosis of BHD syndrome. When we encounter cancer of unknown primary with multiple pulmonary cysts in a patient with a history of pneumothorax, thorough imaging of the kidneys and genetic testing for BHD syndrome is necessary.
一位 60 岁女性因不明原发灶的多处肺和骨转移而就诊。胸部 CT 图像显示多个肺囊肿,主要位于中、下叶。她还有气胸病史。化疗和放疗 4 年后,双侧肾脏最终出现多个富血管性肿瘤,提示存在 Birt-Hogg-Dubé(BHD)综合征的可能。基因检测显示纤维瘤素突变,这证实了 BHD 综合征的诊断。当我们遇到有气胸病史的不明原发灶癌症患者伴多发肺囊肿时,需要对肾脏进行全面成像和 BHD 综合征的基因检测。