de Visser M, Ongerboer de Visser B W, Verbeeten B
Department of Neurology, Academic Medical Center, Amsterdam, The Netherlands.
Eur Neurol. 1988;28(3):135-8. doi: 10.1159/000116249.
Five patients with monomelic spinal muscular atrophy are described. Clinical features included insidious onset of wasting and weakness of one limb, lack of involvement of the cranial nerves, brain stem, pyramidal tracts and sensory system, and a stable condition over a period of 4-20 years. Clinical findings, electromyography and/or muscle biopsy were consistent with anterior horn cell lesion. Central cavities were excluded by magnetic resonance imaging studies of the spinal cord. Computed tomography of skeletal musculature and electromyography indicated more diffuse lower motor neuron involvement by revealing abnormalities in clinically unaffected muscles in 4 of the 5 patients. Myokymic discharges were found in the affected limb of 1 patient.
本文描述了5例单肢型脊髓性肌萎缩患者。临床特征包括:一侧肢体隐匿性起病的消瘦和无力,不累及颅神经、脑干、锥体束和感觉系统,病情在4至20年期间保持稳定。临床检查、肌电图和/或肌肉活检结果均与前角细胞病变相符。脊髓磁共振成像研究排除了中央空洞。骨骼肌计算机断层扫描和肌电图显示,5例患者中有4例在临床未受累的肌肉中发现异常,提示下运动神经元受累更为广泛。1例患者在受累肢体发现肌束震颤放电。