Regenbogen Claudia, Braunisch Matthias Christoph, Schmaderer Christoph, Heemann Uwe
Department of Nephrology, Technical University of Munich, School of Medicine, Klinikum rechts der Isar, Munich, Germany.
Cardiovasc Diagn Ther. 2021 Apr;11(2):661-671. doi: 10.21037/cdt-20-845.
Fabry disease (FD) is a rare X chromosomally transmitted lysosomal storage disorders with an absence or deficiency of the enzyme alpha-galactosidase. The deposition of globotriaosylceramide (Gb3) may cause damage to all organs, particularly brain, heart and kidney. While acroparaesthesia, hypo- or anhydrosis and diarrhoea are the main symptoms in childhood, cardiac involvement with left ventricular hypertrophy (LVH), renal insufficiency, diffuse pain attacks and apoplexy are the main symptoms in adulthood. Regular examinations are necessary to record organ involvement and its progression. A major challenge is therefore to make a diagnosis at an early disease stage. This is the only way that treatment can be started if there is an indication. If FD is suspected, alpha-galactosidase should be tested in male patients and genetic testing should be performed in females to confirm the diagnosis. Since 2001, enzyme replacement therapy (ERT) has been available as a causal therapy. In 2016, chaperone therapy with the drug Migalastat was approved in the European Union, which leads to stabilisation of the defective alpha-galactosidase. Studies on gene therapy to cure FD in phase I/II. This review summarizes which patient should be screened, how to confirm the diagnosis and which examinations should be performed in FD patients during the course of the disease.
法布里病(FD)是一种罕见的X染色体隐性遗传的溶酶体贮积症,因缺乏α-半乳糖苷酶所致。球三糖基神经酰胺(Gb3)的沉积可损害所有器官,尤其是脑、心脏和肾脏。儿童期主要症状为肢端感觉异常、少汗或无汗及腹泻,成年期主要症状为心脏受累伴左心室肥厚(LVH)、肾功能不全、弥漫性疼痛发作和中风。定期检查对于记录器官受累情况及其进展很有必要。因此,一个主要挑战是在疾病早期做出诊断。这是有指征时能够开始治疗的唯一途径。如果怀疑患有FD,男性患者应检测α-半乳糖苷酶,女性患者应进行基因检测以确诊。自2001年以来,酶替代疗法(ERT)已作为一种病因治疗方法应用。2016年,药物米加司他的伴侣疗法在欧盟获批,该疗法可使缺陷型α-半乳糖苷酶稳定。治疗FD的基因疗法正处于I/II期研究阶段。本综述总结了哪些患者应接受筛查、如何确诊以及在FD患者病程中应进行哪些检查。