Suppr超能文献

成人发病型 Brown-Vialetto-Van Laere 综合征三例:SLC52A3 基因突变及 MRI 异常

Three cases of adult-onset Brown-Vialetto-Van Laere syndrome: Novel variants in SLC52A3 gene and MRI abnormalities.

机构信息

Univ. Lille, Inserm, CHU Lille, U1172 - LilNCog - Lille Neuroscience & Cognition, F-59000 Lille, France; Neurology Department, Lille University Medical Center, Lille, France.

Univ. Lille, Inserm, CHU Lille, U1172 - LilNCog - Lille Neuroscience & Cognition, F-59000 Lille, France; Neuroradiology Department, Lille University Medical Center, Lille, France.

出版信息

Neuromuscul Disord. 2021 Aug;31(8):752-755. doi: 10.1016/j.nmd.2021.06.009. Epub 2021 Jun 26.

Abstract

Brown-Vialetto-Van Laere syndrome is a rare, autosomal, recessive neurological condition caused by variants in the riboflavin transporter genes SLC52A2 and SLC52A3. Here, we report on three cases. Case 1 was a 35-year-old woman from a consanguineous family who presented with progressive deafness, subacute multiple cranial nerve impairments (III, VII, IX, XII), and MRI abnormalities (including as hypersignal from the cranial nerves). The patient was homozygous for a novel SLC52A3variant. Case 2 was the woman's brother, who presented similar symptoms. Case 3 was an 18-year-old woman experiencing progressive hearing loss, bilateral steppage gait and a cranial nerves impairment (VII and XII). MRI revealed hypersignal in the root nerves and cauda equina. A novel heterozygous variant in SLC52A3 was identified. A subacute history of polyradiculoneuropathy along with progressive deafness, cranial nerve impairment, and MRI abnormalities should raise suspicion for Brown-Vialetto-Van Laere syndrome.

摘要

Brown-Vialetto-Van Laere 综合征是一种罕见的常染色体隐性遗传性神经疾病,由核黄素转运基因 SLC52A2 和 SLC52A3 的变异引起。本文报告了 3 例病例。病例 1 是一名来自近亲家庭的 35 岁女性,表现为进行性耳聋、亚急性多发性颅神经损伤(III、VII、IX、XII)和 MRI 异常(包括颅神经高信号)。患者为 SLC52A3 新型纯合变异。病例 2 是该女性的兄弟,表现出相似的症状。病例 3 是一名 18 岁女性,表现为进行性听力损失、双侧跨步态和颅神经损伤(VII 和 XII)。MRI 显示神经根和马尾高信号。发现 SLC52A3 的新型杂合变异。具有亚急性多发性神经根神经病病史、进行性耳聋、颅神经损伤和 MRI 异常的患者应怀疑为 Brown-Vialetto-Van Laere 综合征。

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验