Ahmed Selim, Saifuddin Mohd Syafiek, Ng Chiak Yot, Salwati Nik Fatimah, Hayati Firdaus, Ismail Suseela
Paediatric Department, Medical Based Department, Faculty of Medicine & Health Science, Universiti Malaysia Sabah, Kota Kinabalu, Sabah, Malaysia.
Department of Radiology, Hospital Sultanah Bahiyah, Alor Setar, Kedah.
Radiol Case Rep. 2021 Aug 26;16(11):3289-3294. doi: 10.1016/j.radcr.2021.07.081. eCollection 2021 Nov.
Enteric duplications (EDs) are rare congenital anomalies that result from defect during embryonic development of the gut. Although EDs can literally occur at any part of the gastrointestinal tract, ileocecal duplication is the commonest type followed by colorectal type. Morphologically, EDs are mostly cystic in nature; tubular duplications are uncommon. We report radiological diagnostic challenges encountered in dealing with a 10 month-old infant who presented with chronic constipation, progressive abdominal distension, and voiding difficulty for several weeks followed by colicky abdominal pain for three days. After a series of radiological procedures, a diagnosis of tubular colorectal duplication was made. The duplicated segment was loaded with impacted feces which exerted pressure effect on the rectum and urinary bladder. The case was treated surgically through laparoscopic procedure that included fenestration and stapling of the duplicated bowel followed by irrigation. Postoperatively, the child was followed up half-yearly for three years and was found to remain symptom-free. This case exemplifies the challenges a radiologist may experience while dealing with a case presenting with features of as acute-on-chronic intestinal obstruction and voiding difficulty.
肠道重复畸形(EDs)是一种罕见的先天性异常,由肠道胚胎发育过程中的缺陷引起。尽管EDs实际上可发生于胃肠道的任何部位,但回盲部重复畸形是最常见的类型,其次是结直肠型。从形态学上讲,EDs大多为囊性;管状重复畸形并不常见。我们报告了在处理一名10个月大婴儿时遇到的放射学诊断挑战,该婴儿出现慢性便秘、进行性腹胀、排尿困难数周,随后出现绞痛性腹痛三天。经过一系列放射学检查后,诊断为管状结直肠重复畸形。重复段充满了嵌顿的粪便,对直肠和膀胱产生了压迫作用。该病例通过腹腔镜手术进行治疗,包括对重复肠段进行开窗和吻合,随后进行冲洗。术后,对该患儿进行了为期三年的半年一次随访,发现其一直无症状。该病例体现了放射科医生在处理表现为急慢性肠梗阻和排尿困难特征的病例时可能遇到的挑战。