MacDermot K D, Walker R W
Clinical Research Centre, Harrow, UK.
J Neurol Neurosurg Psychiatry. 1987 Oct;50(10):1342-7. doi: 10.1136/jnnp.50.10.1342.
A syndrome is described, consisting of severe neurogenic distal wasting, generalised muscle weakness, absent ankle reflexes, pyramidal signs, mental retardation, optic atrophy and retinal colloid bodies. A sural nerve biopsy from one case showed loss of nerve fibres suggesting the diagnosis of hereditary motor and sensory neuropathy. Progression of the disorder was very slow, all patients still being able to walk more than 20 years after the onset. The persons affected with this syndrome were two brothers and their female cousin from a large Gujerati pedigree where consanguinity was high. Autosomal recessive inheritance is therefore suggested.
描述了一种综合征,其特征包括严重的神经源性远端消瘦、全身性肌无力、踝反射消失、锥体束征、智力发育迟缓、视神经萎缩和视网膜胶体小体。对其中一例患者进行的腓肠神经活检显示神经纤维缺失,提示遗传性运动和感觉神经病的诊断。该疾病进展非常缓慢,所有患者在发病20多年后仍能行走。受此综合征影响的患者为来自一个近亲结婚率很高的大型古吉拉特家族谱系中的两兄弟及其女性堂妹。因此提示为常染色体隐性遗传。