Kasai Yuka, Aoki Ryoji, Nagano Nobuhiko, Kaneda Hide, Koshinaga Tsugumichi, Morioka Ichiro
Department of Pediatrics and Child Health, Nihon University School of Medicine.
Department of Pediatric Surgery, Nihon University School of Medicine.
J Nippon Med Sch. 2023 Feb 1;89(6):623-628. doi: 10.1272/jnms.JNMS.2022_89-606. Epub 2021 Nov 26.
The site of perforation is difficult to identify preoperatively in many cases with spontaneous perforation of congenital biliary dilatation (CBD). We report a case of spontaneous perforation of CBD in which the perforation site was identified preoperatively using thin-slice contrast-enhanced computed tomography (CT). The patient was a girl aged 1 year and 4 months. She was admitted to our hospital because of vomiting and diarrhea that had continued for 3 days prior to admission. Abdominal contrast CT on admission showed dilated common bile duct, thickening of the gall bladder wall, and marked ascites. In addition, an area of low density with a diameter of 1 cm was detected near the neck of the gallbladder. We evaluated the area via thin-slice contrast-enhanced CT and detected a defect in the wall of the bile duct. Cholangiography revealed abnormal confluence of the pancreaticobiliary duct and a protein plug in the common duct. A diagnosis of CBD with perforation of the bile duct was made, and surgery was performed. The intraoperative findings matched that seen on the enhanced CT. There are some reports of pseudocysts and fluid retention around the perforation site; however, no reports are found in which the perforation site was confirmed by preoperative CT. If localized fluid retention is observed in cases with biliary perforation, confirmation with thin-slice contrast-enhanced CT might be useful for identifying the perforation site.
在许多先天性胆管扩张症(CBD)自发性穿孔的病例中,术前很难确定穿孔部位。我们报告一例CBD自发性穿孔病例,术前通过薄层增强计算机断层扫描(CT)确定了穿孔部位。患者为一名1岁4个月的女孩。因入院前持续3天的呕吐和腹泻入院。入院时腹部增强CT显示胆总管扩张、胆囊壁增厚和大量腹水。此外,在胆囊颈部附近检测到一个直径1 cm的低密度区域。我们通过薄层增强CT对该区域进行评估,检测到胆管壁有缺损。胆管造影显示胰胆管异常汇合以及胆总管内有蛋白栓。诊断为CBD伴胆管穿孔,并进行了手术。术中所见与增强CT所见相符。有一些关于穿孔部位周围假性囊肿和液体潴留的报道;然而,未发现术前CT确诊穿孔部位的报道。如果在胆管穿孔病例中观察到局限性液体潴留,通过薄层增强CT进行确认可能有助于确定穿孔部位。