University of Murcia, Murcia, Spain.
Institut Curie, UMR144, Structure and Membrane Compartments, PSL Research University, CNRS, 75005, Paris, France.
Cell Mol Life Sci. 2021 Dec 18;79(1):47. doi: 10.1007/s00018-021-04053-9.
Mahogunin Ring Finger 1 (MGRN1) is an E3-ubiquitin ligase absent in dark-furred mahoganoid mice. We investigated the mechanisms of hyperpigmentation in Mgrn1-null melan-md1 melanocytes, Mgrn1-KO cells obtained by CRISPR-Cas9-mediated knockdown of Mgrn1 in melan-a6 melanocytes, and melan-a6 cells depleted of MGRN1 by siRNA treatment. Mgrn1-deficient melanocytes showed higher melanin content associated with increased melanosome abundance and higher fraction of melanosomes in highly melanized maturation stages III-IV. Expression, post-translational processing and enzymatic activity of the rate-limiting melanogenic enzyme tyrosinase measured in cell-free extracts were comparable in control and MGRN1-depleted cells. However, tyrosinase activity measured in situ in live cells and expression of genes associated with regulation of pH increased upon MGRN1 repression. Using pH-sensitive fluorescent probes, we found that downregulation of MGRN1 expression in melanocytes and melanoma cells increased the pH of acidic organelles, including melanosomes, strongly suggesting a previously unknown role of MGRN1 in the regulation of melanosomal pH. Among the pH regulatory genes upregulated by Mgrn1 knockdown, we identified those encoding several subunits of the vacuolar adenosine triphosphatase V-ATPase (mostly Atp6v0d2) and a calcium channel of the transient receptor potential channel family, Mucolipin 3 (Mcoln3). Manipulation of expression of the Mcoln3 gene showed that overexpression of Mcoln3 played a significant role in neutralization of the pH of acidic organelles and activation of tyrosinase in MGRN1-depleted cells. Therefore, lack of MGRN1 led to cell-autonomous stimulation of pigment production in melanocytes mostly by increasing tyrosinase specific activity through neutralization of the melanosomal pH in a MCOLN3-dependent manner.
Mahogunin 环指蛋白 1(MGRN1)是一种 E3-泛素连接酶,在深褐色毛发的 mahoganoid 小鼠中缺失。我们研究了 Mgrn1 缺失的 melan-md1 黑素细胞、CRISPR-Cas9 介导的 MGRN1 敲低获得的 Mgrn1-KO 细胞以及经 siRNA 处理耗尽 MGRN1 的 melan-a6 细胞中过度色素沉着的机制。缺乏 Mgrn1 的黑素细胞表现出更高的黑色素含量,与黑色素体丰度增加和高度黑素化成熟阶段 III-IV 中的黑色素体比例更高有关。在无细胞提取物中测量的限速黑色素生成酶酪氨酸酶的表达、翻译后加工和酶活性在对照和 MGRN1 耗尽的细胞中是可比的。然而,在活细胞中原位测量的酪氨酸酶活性和与 pH 调节相关的基因表达在 MGRN1 抑制时增加。使用 pH 敏感荧光探针,我们发现黑素细胞和黑色素瘤细胞中 MGRN1 表达的下调增加了酸性细胞器的 pH,包括黑色素体,这强烈表明 MGRN1 在调节黑色素体 pH 方面具有以前未知的作用。在 Mgrn1 敲低上调的 pH 调节基因中,我们鉴定出编码几种空泡型三磷酸腺苷酶 V-ATPase(主要是 Atp6v0d2)和瞬时受体电位通道家族钙通道的基因,Mucolipin 3(Mcoln3)。对 Mcoln3 基因表达的操纵表明,Mcoln3 的过表达在中和 MGRN1 耗尽细胞中酸性细胞器的 pH 以及激活酪氨酸酶方面发挥了重要作用。因此,缺乏 MGRN1 导致黑素细胞中自主刺激色素生成,主要是通过中和黑色素体 pH 以依赖于 MCOLN3 的方式增加酪氨酸酶的特异性活性。