Suppr超能文献

唐氏综合征相关关节炎(DA):诊断与管理挑战

Down Syndrome-Associated Arthritis (DA): Diagnostic and Management Challenges.

作者信息

Jones Jordan T, Kitchen Jacqueline, Talib Nasreen

机构信息

Division of Rheumatology, Children's Mercy Kansas City, Kansas City, MO, USA.

Division of Pediatrics, Children's Mercy Kansas City, Kansas City, MO, USA.

出版信息

Pediatric Health Med Ther. 2022 Mar 14;13:53-62. doi: 10.2147/PHMT.S282646. eCollection 2022.

Abstract

Down syndrome (DS) is one of the most common birth defects in the United States, the most common genomic disorder of intellectual disability, and results from trisomy 21. This chromosome disorder causes an extensive, heterogenous phenotype that results in a broad presentation of symptoms that includes atlantoaxial instability, congenital heart defects, muscle hypotonia, hypothyroidism, hematologic disorders, recurrent infections, and autoimmune diseases. The autoimmune diseases are caused by immune system dysregulation that results in increased pro-inflammatory cytokines, along with other innate and adaptive immune system dysregulation. This is the likely cause of the increased risk of inflammatory arthritis or Down syndrome-associated arthritis (DA) seen in individuals with DS. Most individuals with DA present with polyarticular (five or more joints with arthritis at presentation of disease), rheumatoid factor and anti-nuclear antibody negative disease that is aggressive with bone and joint damage at presentation. There is notable delay in diagnosis of DA as there are no formal guidelines on screening or monitoring for inflammatory arthritis in individuals with DS. Once diagnosed, and despite aggressive therapy with disease modifying antirheumatic drugs, disease burden is high for those with DA. Therapy can also be challenging for those with DA as many require second and third-line disease modifying therapies. Many also struggle with medication toxicity and ineffectiveness that further causes challenges with management and outcomes. The purpose of this current review is to provide an up-to-date summary of the literature related to DA in children and adolescents with focus on presentation, diagnosis, and management considerations, along with current barriers that inhibit optimal care.

摘要

唐氏综合征(DS)是美国最常见的出生缺陷之一,是最常见的导致智力残疾的基因组疾病,由21号染色体三体性引起。这种染色体疾病会导致广泛的、异质性的表型,从而产生一系列症状,包括寰枢椎不稳定、先天性心脏缺陷、肌张力减退、甲状腺功能减退、血液系统疾病、反复感染和自身免疫性疾病。自身免疫性疾病是由免疫系统失调引起的,导致促炎细胞因子增加,同时伴有其他先天性和适应性免疫系统失调。这可能是唐氏综合征患者中炎性关节炎或唐氏综合征相关关节炎(DA)风险增加的原因。大多数DA患者表现为多关节(疾病发作时五个或更多关节患有关节炎)、类风湿因子和抗核抗体阴性疾病,疾病发作时对骨骼和关节有侵袭性损害。由于没有关于唐氏综合征患者炎性关节炎筛查或监测的正式指南,DA的诊断明显延迟。一旦确诊,尽管使用改善病情抗风湿药物进行积极治疗,但DA患者的疾病负担仍然很高。对于DA患者来说,治疗也具有挑战性,因为许多患者需要二线和三线改善病情的治疗。许多患者还面临药物毒性和无效的问题,这进一步给管理和治疗结果带来挑战。本综述的目的是提供有关儿童和青少年DA的最新文献总结,重点关注临床表现、诊断和管理考虑因素,以及目前阻碍最佳治疗的障碍。

相似文献

1
4
Treatment of Down Syndrome-Associated Arthritis with JAK Inhibition.用JAK抑制疗法治疗唐氏综合征相关关节炎。
Case Rep Rheumatol. 2022 Jul 16;2022:4889102. doi: 10.1155/2022/4889102. eCollection 2022.
10
Pharmacotherapeutic Considerations for Individuals with Down Syndrome.唐氏综合征患者的药物治疗考量
Pharmacotherapy. 2017 Feb;37(2):214-220. doi: 10.1002/phar.1880. Epub 2017 Jan 13.

引用本文的文献

1
Expression profile of inflammasome genes in individuals with Down syndrome.唐氏综合症个体中炎性小体基因的表达谱
Genet Mol Biol. 2024 Sep 9;47(4):e20230339. doi: 10.1590/1678-4685-GMB-2023-0339. eCollection 2024.
2
Down Syndrome and Autoimmune Disease.唐氏综合征与自身免疫性疾病。
Clin Rev Allergy Immunol. 2024 Jun;66(3):261-273. doi: 10.1007/s12016-024-08996-2. Epub 2024 Jun 24.
7
Treatment of Down Syndrome-Associated Arthritis with JAK Inhibition.用JAK抑制疗法治疗唐氏综合征相关关节炎。
Case Rep Rheumatol. 2022 Jul 16;2022:4889102. doi: 10.1155/2022/4889102. eCollection 2022.

本文引用的文献

8
Down Syndrome.唐氏综合征
N Engl J Med. 2020 Jun 11;382(24):2344-2352. doi: 10.1056/NEJMra1706537.
9
Down syndrome.唐氏综合征。
Nat Rev Dis Primers. 2020 Feb 6;6(1):9. doi: 10.1038/s41572-019-0143-7.

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验