Lee Yong-Moon, Choi Yoon Seok, Kim Jin-Man
Department of Pathology, College of Medicine, Dankook University, Cheonan 31116, Korea.
Department of Hematology-Oncology, College of Medicine, Ajou University, Suwon 16499, Korea.
Diagnostics (Basel). 2022 Apr 15;12(4):998. doi: 10.3390/diagnostics12040998.
POEMS syndrome (POEMS) is a rare plasma cell clonal paraneoplastic syndrome consisting of polyneuropathy, organomegaly, endocrinopathy, monoclonal protein, and skin changes presenting with idiopathic multicentric Castleman disease (iMCD) histology, the treatment of which has not yet been well established. iMCD is also a distinctive rare non-clonal lymphoproliferative disorder, of which dramatic response to Siltuximab, a monoclonal anti-IL-6 antibody, has been reported recently.
the differential diagnosis between POEMS and iMCD can be very challenging because of the identical histology, overlapping similar symptoms such as polyneuropathy, and vital signs insidiously presented to diagnose POEMS.
here, we report the case of a 53-year-old man with iMCD treated for 8 years developing sequential polyneuropathy, monoclonal gammopathy, and bone lytic lesions, all of which were confirmed after his iMCD achieved complete remission resulting from siltuximab administration and finally confirmed as POEMS.
we describe the clinical ambiguity of disease presenting that we can face in the real world between iMCD and POEMS and emphasise careful, enduring observation lasting several years.
POEMS综合征(POEMS)是一种罕见的浆细胞克隆性副肿瘤综合征,由多发性神经病、器官肿大、内分泌病、单克隆蛋白和皮肤改变组成,其组织学表现为特发性多中心Castleman病(iMCD),目前其治疗方法尚未完全确立。iMCD也是一种独特的罕见非克隆性淋巴增殖性疾病,最近有报道称其对单克隆抗IL-6抗体西妥昔单抗有显著反应。
POEMS和iMCD的鉴别诊断可能极具挑战性,因为它们的组织学相同,存在诸如多发性神经病等重叠的相似症状,且POEMS的生命体征隐匿难以诊断。
在此,我们报告一例53岁男性iMCD患者,接受治疗8年后出现继发性多发性神经病、单克隆丙种球蛋白病和溶骨性病变,在其iMCD因使用西妥昔单抗而完全缓解后,所有这些病变均得到确诊,最终确诊为POEMS。
我们描述了在现实世界中iMCD和POEMS之间疾病表现的临床模糊性,并强调需要进行持续数年的仔细、持久观察。