deCODE genetics/Amgen Inc., Reykjavik, Iceland.
Faculty of Medicine, School of Health Sciences, University of Iceland, Reykjavik, Iceland.
Commun Biol. 2022 Jun 1;5(1):525. doi: 10.1038/s42003-022-03462-1.
The characteristic lobulated nuclear morphology of granulocytes is partially determined by composition of nuclear envelope proteins. Abnormal nuclear morphology is primarily observed as an increased number of hypolobulated immature neutrophils, called band cells, during infection or in rare envelopathies like Pelger-Huët anomaly. To search for sequence variants affecting nuclear morphology of granulocytes, we performed a genome-wide association study using band neutrophil fraction from 88,101 Icelanders. We describe 13 sequence variants affecting band neutrophil fraction at nine loci. Five of the variants are at the Lamin B receptor (LBR) locus, encoding an inner nuclear membrane protein. Mutations in LBR are linked to Pelger-Huët anomaly. In addition, we identify cosegregation of a rare stop-gain sequence variant in LBR and Pelger Huët anomaly in an Icelandic eight generation pedigree, initially reported in 1963. Two of the other loci include genes which, like LBR, play a role in the nuclear membrane function and integrity. These GWAS results highlight the role proteins of the inner nuclear membrane have as important for neutrophil nuclear morphology.
粒细胞的特征性分叶核形态部分取决于核膜蛋白的组成。异常核形态主要表现为感染期间或在罕见的 envelopathies (如 Pelger-Huët 异常)中幼稚中性粒细胞数量增加,称为带状细胞。为了寻找影响粒细胞核形态的序列变异,我们对 88101 名冰岛人进行了全基因组关联研究,使用了带状中性粒细胞分数。我们描述了 9 个位点影响带状中性粒细胞分数的 13 个序列变异。其中 5 个变异位于核膜蛋白 lamin B 受体(LBR)基因座。LBR 基因突变与 Pelger-Huët 异常有关。此外,我们还在一个冰岛八代家系中鉴定到 LBR 中的一个罕见的无义序列变异与 Pelger Huët 异常的共分离,该家系最初于 1963 年报道。其他两个基因座包括与 LBR 一样在核膜功能和完整性中起作用的基因。这些 GWAS 结果突出了核膜蛋白在中性粒细胞核形态中的重要作用。