Behavioral Neuroscience, Ruhr-University Bochum, Bochum D-44780, Germany.
Hum Mol Genet. 2022 Nov 10;31(22):3807-3828. doi: 10.1093/hmg/ddac135.
Fear and anxiety have proven to be essential during the evolutionary process. However, the mechanisms involved in recognizing and categorizing threat probability (i.e. low to high) to elicit the appropriate defensive behavior are yet to be determined. In this study, we investigated the cerebellar contribution in evoking appropriate defensive escape behavior using a purely cerebellar, neurodegenerative mouse model for spinocerebellar ataxia type 6 which is caused by an expanded CAG repeat in exon 47 of the P/Q type calcium channel α1A subunit. These mice overexpress the carboxy terminus (CT) of the P/Q type calcium channel containing an expanded 27 CAG repeat specifically in cerebellar Purkinje cells (CT-longQ27PC). We found that our CT-longQ27PC mice exhibit anxiolytic behavior in the open field, elevated plus maze and light/dark place preference tests, which could be recovered with more threatening conditions such as brighter lighting, meowing sounds and an ultrasound repellent. Their innate fear to find safety in the Barnes maze and visual cliff tests was also diminished with subsequent trials, which could be partially recovered with an ultrasound repellent in the Barnes maze. However, under higher threat conditions such as in the light/dark place preference with ultrasound repellent and in the looming tests, CT-longQ27PC mice responded with higher defensive escape behaviors as controls. Moreover, CT-longQ27PC mice displayed increased levels of CT-labeled aggregates compared with controls. Together these data suggest that cerebellar degeneration by overexpression of CT-longQ27PC is sufficient to impair defensive escape responses in those mice.
恐惧和焦虑已被证明在进化过程中是必不可少的。然而,参与识别和分类威胁概率(即低到高)以引发适当防御行为的机制仍有待确定。在这项研究中,我们使用一种纯粹的小脑、神经退行性小脑共济失调 6 型的小鼠模型来研究小脑在引发适当防御性逃避行为中的作用,该模型是由 P/Q 型钙通道α1A 亚基外显子 47 中的 CAG 重复扩增引起的。这些小鼠在小脑浦肯野细胞中特异性过表达含有扩增 27 个 CAG 重复的 P/Q 型钙通道羧基末端(CT)(CT-longQ27PC)。我们发现,我们的 CT-longQ27PC 小鼠在开阔场、高架十字迷宫和明暗偏好测试中表现出焦虑样行为,这些行为可以通过更具威胁性的条件恢复,例如更亮的照明、喵喵声和超声驱虫器。它们在 Barnes 迷宫和视觉悬崖测试中寻找安全的先天恐惧也随着后续试验而减少,这可以部分通过 Barnes 迷宫中的超声驱虫器恢复。然而,在更高的威胁条件下,例如在有超声驱虫器的明暗偏好和迫近测试中,CT-longQ27PC 小鼠的防御性逃避行为与对照组相比反应更高。此外,与对照组相比,CT-longQ27PC 小鼠显示出更高水平的 CT 标记聚集体。这些数据表明,CT-longQ27PC 的过度表达导致小脑退化足以损害这些小鼠的防御性逃避反应。