Department of Biochemistry and Molecular Biology, University of Calgary, Calgary, AB T2N 4N1, Canada.
Molecular Biosciences, Northwestern University, Evanston, IL 60208, USA.
Genetics. 2022 Jul 30;221(4). doi: 10.1093/genetics/iyac093.
Parasitic nematodes are major human and agricultural pests, and benzimidazoles are amongst the most important broad-spectrum anthelmintic drug class used for their control. Benzimidazole resistance is now widespread in many species of parasitic nematodes in livestock globally and an emerging concern for the sustainable control of human soil-transmitted helminths. β-tubulin is the major benzimidazole target, although other genes may influence resistance. Among the 6 Caenorhabditis elegans β-tubulin genes, loss of ben-1 causes resistance without other apparent defects. Here, we explored the genetics of C. elegans β-tubulin genes in relation to the response to the benzimidazole derivative albendazole. The most highly expressed β-tubulin isotypes, encoded by tbb-1 and tbb-2, were known to be redundant with each other for viability, and their products are predicted not to bind benzimidazoles. We found that tbb-2 mutants, and to a lesser extent tbb-1 mutants, were hypersensitive to albendazole. The double mutant tbb-2 ben-1 is uncoordinated and short, resembling the wild type exposed to albendazole, but the tbb-1 ben-1 double mutant did not show the same phenotypes. These results suggest that tbb-2 is a modifier of albendazole sensitivity. To better understand how BEN-1 mutates to cause benzimidazole resistance, we isolated mutants resistant to albendazole and found that 15 of 16 mutations occurred in the ben-1 coding region. Mutations ranged from likely nulls to hypomorphs, and several corresponded to residues that cause resistance in other organisms. Null alleles of ben-1 are albendazole-resistant and BEN-1 shows high sequence identity with tubulins from other organisms, suggesting that many amino acid changes could cause resistance. However, our results suggest that missense mutations conferring resistance are not evenly distributed across all possible conserved sites. Independent of their roles in benzimidazole resistance, tbb-1 and tbb-2 may have specialized functions as null mutants of tbb-1 or tbb-2 were cold or heat sensitive, respectively.
寄生虫线虫是人类和农业的主要害虫,苯并咪唑类药物是用于控制寄生虫线虫的最重要的广谱驱虫药物之一。目前,在全球许多牲畜寄生虫线虫物种中,苯并咪唑类药物耐药性已广泛存在,这对人类土壤传播性蠕虫的可持续控制构成了新的挑战。β-微管蛋白是苯并咪唑类药物的主要靶标,尽管其他基因也可能影响耐药性。在秀丽隐杆线虫的 6 个β-微管蛋白基因中,ben-1 的缺失会导致耐药性,而没有其他明显的缺陷。在这里,我们研究了秀丽隐杆线虫β-微管蛋白基因与苯并咪唑衍生物阿苯达唑反应之间的遗传关系。已知表达量最高的β-微管蛋白同工型由 tbb-1 和 tbb-2 编码,它们在生存能力上彼此冗余,并且它们的产物预计不与苯并咪唑结合。我们发现,tbb-2 突变体,在较小程度上 tbb-1 突变体,对阿苯达唑敏感。双突变体 tbb-2 ben-1 不协调且短小,类似于暴露于阿苯达唑的野生型,但 tbb-1 ben-1 双突变体并未表现出相同的表型。这些结果表明 tbb-2 是阿苯达唑敏感性的修饰因子。为了更好地理解 BEN-1 如何突变导致苯并咪唑耐药,我们分离出对阿苯达唑耐药的突变体,发现 16 个突变中有 15 个发生在 ben-1 编码区。突变范围从可能的无效突变到亚效突变,其中几个突变与其他生物体中引起耐药的残基相对应。ben-1 的无效等位基因对阿苯达唑耐药,并且 BEN-1 与其他生物体的微管蛋白具有高度序列同一性,这表明许多氨基酸变化都可能导致耐药性。然而,我们的结果表明,赋予耐药性的错义突变并非均匀分布在所有可能的保守位点上。无论它们在苯并咪唑耐药性中的作用如何,tbb-1 和 tbb-2 都可能具有特殊功能,因为 tbb-1 或 tbb-2 的缺失突变体分别对冷或热敏感。