School of Medicine, National Yang Ming Chiao Tung University, Taipei, Taiwan.
Department of Radiology, Taichung Veterans General Hospital, Taichung, Taiwan.
Sci Rep. 2022 Jun 22;12(1):10499. doi: 10.1038/s41598-022-14531-0.
Differentiation cerebellar multiple systemic atrophy (MSA-C) from spinocerebellar ataxia (SCA) is important. The "hot cross bun" sign (HCBS) at pons and magnetic resonance spectroscopy (MRS) are helpful. However, the prevalence of HCBS and the alteration of cerebellar MRS parameters are evolving with disease progression. We hypothesized that since the HCBS and MRS are evolving with time, different parameters for differentiation of MSA-C and SCA are required at different disease stages. The aim of this study was to evaluate the HCBS and MRS changes in patients with MSA-C and SCA at different disease stages. A total of 398 patients with molecularly confirmed SCA (SCA1, 2, 3, 6, 17) and 286 patients diagnosed with probable MSA-C (without mutations in SCA1, 2, 3, 6, 17 genes), who had received brain magnetic resonance imaging (MRI) and MRS from January 2000 to January 2020, were recruited. Twenty-five patients were molecularly identified as having SCA1, 68 as SCA2, 253 as SCA3, 34 as SCA6, and 18 as SCA17. We compared their clinical parameters and neuroimaging features at different disease stages. The presence of HCBS was assessed using an axial T2 fast spin-echo or FLAIR sequence. Proton MRS was recorded with voxel of interest focusing on cerebellar hemispheres and cerebellar vermis and avoiding cerebrospinal fluid spaces space using a single-voxel stimulated echo acquisition mode sequence. We found that patients with MSA-C tend to have a higher prevalence of pontine HCBS, worse Scale for the Assessment and Rating of Ataxia scores, lower cerebellar N-acetyl aspartate (NAA)/creatinine (Cr), and choline (Cho)/Cr, compared to patients with SCA at corresponding disease stages. In MSA-C patients with a disease duration < 1 year and without pontine HCBS, a cerebellar NAA/Cr ≤ 0.79 is a good indicator of the possibility of MSA-C. By using the pontine HCBS and cerebellar MRS, discerning MSA-C from SCA became possible. This study provides cutoff values of MRS to serve as clues in differentiating MSA-C from SCAs.
从多系统萎缩(MSA)中区分小脑型(MSA-C)与脊髓小脑性共济失调(SCA)很重要。桥脑的“十字面包”征(HCBS)和磁共振波谱(MRS)很有帮助。然而,随着疾病的进展,HCBS 的发生率和小脑 MRS 参数的变化也在不断变化。我们假设由于 HCBS 和 MRS 随时间而变化,因此在不同的疾病阶段需要使用不同的参数来区分 MSA-C 和 SCA。本研究旨在评估不同疾病阶段 MSA-C 和 SCA 患者的 HCBS 和 MRS 变化。共纳入 398 例经分子证实的 SCA(SCA1、2、3、6、17)患者和 286 例疑诊 MSA-C 患者(SCA1、2、3、6、17 基因突变阴性),这些患者于 2000 年 1 月至 2020 年 1 月期间接受了脑部磁共振成像(MRI)和 MRS 检查。25 例患者被确认为 SCA1,68 例为 SCA2,253 例为 SCA3,34 例为 SCA6,18 例为 SCA17。我们比较了他们在不同疾病阶段的临床参数和神经影像学特征。采用轴位 T2 快速自旋回波或 FLAIR 序列评估 HCBS 的存在。使用单容积激发回波采集模式序列,在感兴趣容积(ROI)聚焦于小脑半球和小脑蚓部,避免脑脊液空间,记录质子 MRS。我们发现,与相应疾病阶段的 SCA 患者相比,MSA-C 患者更倾向于出现较高的桥脑 HCBS 发生率、更差的共济失调评估量表评分、更低的小脑 N-乙酰天冬氨酸(NAA)/肌酐(Cr)和胆碱(Cho)/Cr。在疾病持续时间<1 年且无桥脑 HCBS 的 MSA-C 患者中,小脑 NAA/Cr≤0.79 是 MSA-C 可能性的良好指标。通过使用桥脑 HCBS 和小脑 MRS,能够区分 MSA-C 和 SCA。本研究提供了 MRS 的截止值,可作为区分 MSA-C 和 SCA 的线索。