Surgery, Makunda Christian Leprosy and General Hospital, Karimganj, Assam, India
Anaesthesia, Makunda Christian Leprosy and General Hospital, Karimganj, Assam, India.
BMJ Case Rep. 2022 Jul 14;15(7):e248221. doi: 10.1136/bcr-2021-248221.
A teenage girl presented to our remote rural hospital with history of massive haemoptysis. A CT scan showed a spherical lesion in the right lung. Exploratory thoracotomy was performed with a provisional diagnosis of pulmonary hydatid cyst. Intraoperative findings were consistent with intrapulmonary teratoma and this was confirmed by a histopathological diagnosis of mature teratoma. Four years later, the patient presented again with recurrence of haemoptysis and a right middle lobectomy was performed. We present a report of successful management of this patient with 20-year follow-up since the first surgery, describe the pathology of this rare condition and the procedures used to treat it. We also discuss the social and economic factors that affect decision making in the management of rare conditions in remote rural areas among poor communities that are usually referred to tertiary hospitals and suggest modifications to protocols to provide effective treatment in spite of resource constraints.
一位少女因大量咯血到我们偏远的农村医院就诊。CT 扫描显示右肺有一个球形病变。进行了开胸探查术,初步诊断为肺包虫囊肿。术中所见与肺内畸胎瘤一致,组织病理学诊断也证实为成熟畸胎瘤。四年后,患者再次出现咯血,行右肺中叶切除术。我们报告了一例成功治疗该患者的病例,该患者自第一次手术后进行了 20 年的随访,描述了这种罕见疾病的病理特征和治疗方法。我们还讨论了在向三级医院转诊的贫困社区中,影响偏远农村地区罕见疾病管理决策的社会和经济因素,并提出了修改方案以克服资源限制,提供有效的治疗。