Moerman P, Fryns J P, Devlieger H, Van Assche A, Lauweryns J
Am J Med Genet. 1987 May;27(1):213-8. doi: 10.1002/ajmg.1320270124.
We describe two infants dying neonatally of respiratory failure despite all attempts at resuscitation. The most striking finding at autopsy was eventration and reduced muscle content of the diaphragm. Microscopic examination of the skeletal muscles, in combination with retrospective evaluation of the family history, disclosed severe X-linked centronuclear myopathy in the first patient and congenital myotonic dystrophy in the second. These disorders are probably more frequent than reported before. Their identification is important, not only for genetic counseling of the involved families but also for providing the neonatologist a sufficient explanation for the failure of resuscitation.
我们描述了两名婴儿,尽管进行了所有复苏尝试,仍在新生儿期死于呼吸衰竭。尸检时最显著的发现是膈肌膨出和膈肌肌肉含量减少。对骨骼肌进行显微镜检查,并结合家族史的回顾性评估,发现第一名患者患有严重的X连锁中央核性肌病,第二名患者患有先天性肌强直性营养不良。这些疾病可能比以前报道的更为常见。它们的诊断很重要,不仅对于相关家庭的遗传咨询,而且对于为新生儿科医生提供复苏失败的充分解释也很重要。