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免疫功能正常患者中与周围囊肿相关的肺嗜酸性细胞增多症:一例报告

Pulmonary Malakoplakia Associated with Peripheral Cysts in an Immunocompetent Patient: A Case Report.

作者信息

Corrêa Liana Ferreira, da Silva Thiago Krieger Bento, Camargo Spencer Marcantonio, Furian Bianca Canela

机构信息

Department of Pulmonology, Hospital Santa Casa de Misericórdia de Porto Alegre, Porto Alegre, Brasil.

Department of Thoracic Radiology, Hospital Santa Casa de Misericórdia de Porto Alegre, Porto Alegre, Brasil.

出版信息

J Chest Surg. 2022 Oct 5;55(5):422-424. doi: 10.5090/jcs.22.018. Epub 2022 Sep 7.

DOI:10.5090/jcs.22.018
PMID:36068965
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC9579848/
Abstract

Pulmonary malakoplakia is a rare lung lesion more frequently found in immunocompromised patients than in immunocompetent individuals. In this study, we report the challenging case of a young immunocompetent patient with an irregular pulmonary nodule with peripheral cysts who, after undergoing surgery, was diagnosed with malakoplakia. Due to the rarity of the disease and the similarity of this condition to malignant neoplasms, cytopathological or histopathological examinations are necessary for the correct diagnosis. A description of pulmonary malakoplakia with peripheral cysts has not been previously published in the literature.

摘要

肺软斑病是一种罕见的肺部病变,在免疫功能低下的患者中比在免疫功能正常的个体中更常见。在本研究中,我们报告了一例具有挑战性的病例,一名免疫功能正常的年轻患者有一个伴有周边囊肿的不规则肺结节,在接受手术后被诊断为软斑病。由于该疾病罕见且这种情况与恶性肿瘤相似,因此进行细胞病理学或组织病理学检查对于正确诊断是必要的。此前文献中尚未发表过伴有周边囊肿的肺软斑病的描述。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1a6a/9579848/3bc4d5cc8c96/jcs-55-5-422-f2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1a6a/9579848/b7c0d63170e9/jcs-55-5-422-f1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1a6a/9579848/3bc4d5cc8c96/jcs-55-5-422-f2.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1a6a/9579848/b7c0d63170e9/jcs-55-5-422-f1.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/1a6a/9579848/3bc4d5cc8c96/jcs-55-5-422-f2.jpg

相似文献

1
Pulmonary Malakoplakia Associated with Peripheral Cysts in an Immunocompetent Patient: A Case Report.免疫功能正常患者中与周围囊肿相关的肺嗜酸性细胞增多症:一例报告
J Chest Surg. 2022 Oct 5;55(5):422-424. doi: 10.5090/jcs.22.018. Epub 2022 Sep 7.
2
Malakoplakia presenting as Pleuropulmonary masses: A rare clinical, radiological and histopathological diagnosis.表现为胸膜肺部肿块的软斑病:一种罕见的临床、放射学和组织病理学诊断。
Radiol Case Rep. 2021 Sep 8;16(12):3859-3863. doi: 10.1016/j.radcr.2021.06.070. eCollection 2021 Dec.
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Indian J Pathol Microbiol. 2011 Jan-Mar;54(1):133-5. doi: 10.4103/0377-4929.77366.
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Cecal malakoplakia: A case report.盲肠马氏斑:一例报告。
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Perianal cutaneous malakoplakia in an immunocompetent patient.
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Int J Clin Exp Pathol. 2018 Aug 1;11(8):4153-4157. eCollection 2018.
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本文引用的文献

1
Malakoplakia presenting as Pleuropulmonary masses: A rare clinical, radiological and histopathological diagnosis.表现为胸膜肺部肿块的软斑病:一种罕见的临床、放射学和组织病理学诊断。
Radiol Case Rep. 2021 Sep 8;16(12):3859-3863. doi: 10.1016/j.radcr.2021.06.070. eCollection 2021 Dec.
2
Malakoplakia in Thoracic Transplant Recipients.胸段移植受者的软斑病
Transplant Proc. 2019 Apr;51(3):871-874. doi: 10.1016/j.transproceed.2018.11.008. Epub 2019 Jan 8.
3
Pulmonary malakoplakia secondary to Rhodococcus equi infection mimicking a lung neoplasm in a lung transplant recipient.
肺马尔尼菲青霉病继发于马红球菌感染,在肺移植受者中模拟肺部肿瘤。
Am J Transplant. 2019 Feb;19(2):597-600. doi: 10.1111/ajt.15045. Epub 2018 Sep 4.
4
Malakoplakia Presenting as an Endobronchial Lesion in a Human Immunodeficiency Virus-Positive Man.以支气管内病变形式出现的软斑病见于一名人类免疫缺陷病毒阳性男性。
Am J Med Sci. 2017 Aug;354(2):211-212. doi: 10.1016/j.amjms.2016.10.006. Epub 2016 Oct 27.
5
Pulmonary malakoplakia: a case report and review of the literature.肺软斑症:一例病例报告及文献复习
Tuberk Toraks. 2014;62(3):248-52.
6
Pulmonary malacoplakia at early stage: use of polymerase chain reaction for detection of Rhodococcus equi.肺部软疣病早期:聚合酶链反应检测马红球菌。
Int J Immunopathol Pharmacol. 2012 Jul-Sep;25(3):703-12. doi: 10.1177/039463201202500316.
7
Pulmonary malakoplakia: a rare presentation mimicking extensive stage IV lung cancer.
Eur Respir J. 2011 Oct;38(4):983-5. doi: 10.1183/09031936.00002911.
8
Pulmonary malakoplakia: a report of two cases.肺软斑病:两例报告
Indian J Pathol Microbiol. 2011 Jan-Mar;54(1):133-5. doi: 10.4103/0377-4929.77366.
9
Pulmonary malakoplakia diagnosed by fine needle aspiration. A case report.
Acta Cytol. 1997 Nov-Dec;41(6):1833-8. doi: 10.1159/000333197.