Molecular Medicine Research Group, Eotvos Lorand Research Network and Semmelweis University, Budapest, Hungary.
Hereditary Tumours Research Group, Eotvos Lorand Research Network and Semmelweis University, Budapest, Hungary.
PLoS One. 2022 Dec 1;17(12):e0277299. doi: 10.1371/journal.pone.0277299. eCollection 2022.
Quantitative PCR (qPCR) is used for the determination of gene copy number (GCN). GCNs contribute to human disorders, and characterize copy number variation (CNV). The single laboratory method validations of duplex qPCR assays with hydrolysis probes on CYP21A1P and CYP21A2 genes, residing a CNV (RCCX CNV) and related to congenital adrenal hyperplasia, were performed using 46 human genomic DNA samples. We also performed the verifications on 5 qPCR assays for the genetic elements of RCCX CNV; C4A, C4B, CNV breakpoint, HERV-K(C4) CNV deletion and insertion alleles. Precision of each qPCR assay was under 1.01 CV%. Accuracy (relative error) ranged from 4.96±4.08% to 9.91±8.93%. Accuracy was not tightly linked to precision, but was significantly correlated with the efficiency of normalization using the RPPH1 internal reference gene (Spearman's ρ: 0.793-0.940, p>0.0001), ambiguity (ρ = 0.671, p = 0.029) and misclassification (ρ = 0.769, p = 0.009). A strong genomic matrix effect was observed, and target-singleplex (one target gene in one assay) qPCR was able to appropriately differentiate 2 GCN from 3 GCN at best. The analysis of all GCNs from the 7 qPCR assays using a multiplex approach increased the resolution of differentiation, and produced 98% of GCNs unambiguously, and all of which were in 100% concordance with GCNs measured by Southern blot, MLPA and aCGH. We conclude that the use of an internal (in one assay with the target gene) reference gene, the use of allele-specific primers or probes, and the multiplex approach (in one assay or different assays) are crucial for GCN determination using qPCR or other methods.
实时荧光定量聚合酶链式反应(qPCR)用于测定基因拷贝数(GCN)。GCN 与人类疾病有关,并描述了拷贝数变异(CNV)。使用 46 个人基因组 DNA 样本对 CYP21A1P 和 CYP21A2 基因上水解探针的双 qPCR 测定法进行了单实验室方法验证,这些基因存在 CNV(RCCX CNV),与先天性肾上腺增生有关。我们还对 RCCX CNV 的遗传元件的 5 个 qPCR 测定法进行了验证;C4A、C4B、CNV 断点、HERV-K(C4)CNV 缺失和插入等位基因。每个 qPCR 测定法的精密度均低于 1.01%CV。准确性(相对误差)范围为 4.96±4.08%至 9.91±8.93%。准确性与精密度没有紧密联系,但与使用 RPPH1 内参基因进行归一化的效率显著相关(Spearman's ρ:0.793-0.940,p>0.0001)、歧义(ρ=0.671,p=0.029)和分类错误(ρ=0.769,p=0.009)。观察到强烈的基因组基质效应,并且目标单重(一个测定法中的一个目标基因)qPCR 能够最佳地区分 2 个 GCN 和 3 个 GCN。使用多重方法分析 7 个 qPCR 测定法中的所有 GCN 增加了区分的分辨率,并产生了 98%的 GCN 无歧义,并且所有 GCN 都与 Southern blot、MLPA 和 aCGH 测量的 GCN 完全一致。我们得出结论,使用内部(在一个测定法中与目标基因一起)内参基因、使用等位基因特异性引物或探针以及多重方法(在一个测定法或不同的测定法中)对于使用 qPCR 或其他方法进行 GCN 测定至关重要。