Fox J G
Metabolic Diseases and Chemistry Section, Cadham Provincial Laboratory, Winnipeg, Man.
CMAJ. 1987 Nov 15;137(10):883-8.
The Manitoba Perinatal Screening Program is guided by a committee of medical specialists with skills in the diagnosis and management of disorders of metabolism in the newborn. The program is voluntary and is centralized at Cadham Provincial Laboratory, in Winnipeg. A filter card blood specimen is collected from newborns on discharge from hospital, and a filter card urine sample is collected and mailed to the laboratory by the mother when the infant is about 2 weeks of age. The overall compliance rates for the blood and urine specimens are approximately 100% and 84% respectively. The blood specimen is screened for phenylalanine and other amino acids, thyroxine, galactose, galactose-1-phosphate and biotinidase. The urine specimen is screened for amino acids, including cystine, as well as methylmalonic acid and homocystine. Between 1965 and 1985, 83 cases of metabolic disorders were detected, including 23 cases of primary hypothyroidism, 14 of classic phenylketonuria, 5 of galactosemia variants, 3 of galactosemia, 2 of maple syrup urine disease and 1 of hereditary tyrosinemia. The direct cost per infant screened is $5.50, and the cost:benefit ratio is approximately 7.5:1. Maternal serum alpha-fetoprotein screening is being made available as the necessary supporting clinical facilities become available. On the basis of this experience, the author outlines the components that are important for an effective screening program.
曼尼托巴围产期筛查项目由一个医学专家委员会指导,这些专家具备诊断和管理新生儿代谢紊乱的技能。该项目是自愿参与的,集中在温尼伯的卡德姆省级实验室进行。从新生儿出院时采集滤纸血样,婴儿约2周大时,母亲采集滤纸尿样并邮寄至实验室。血样和尿样的总体合规率分别约为100%和84%。血样筛查苯丙氨酸和其他氨基酸、甲状腺素、半乳糖、1-磷酸半乳糖和生物素酶。尿样筛查氨基酸,包括胱氨酸,以及甲基丙二酸和高胱氨酸。1965年至1985年间,共检测出83例代谢紊乱病例,包括23例原发性甲状腺功能减退、14例经典苯丙酮尿症、5例半乳糖血症变异型、3例半乳糖血症、2例枫糖尿症和1例遗传性酪氨酸血症。每个接受筛查的婴儿的直接成本为5.50美元,成本效益比约为7.5:1。随着必要的辅助临床设施到位,正在开展母血清甲胎蛋白筛查。基于这一经验,作者概述了有效筛查项目的重要组成部分。