Division of Nephrology and Hypertension, Department of Medicine, Mayo Clinic, Rochester, MN, USA.
Division of Pediatric Nephrology and Hypertension, Department of Pediatric Adolescent Medicine, Mayo Clinic, Rochester, MN, USA.
Am J Case Rep. 2023 Feb 27;24:e938889. doi: 10.12659/AJCR.938889.
BACKGROUND Autosomal dominant polycystic kidney disease (ADPKD) is the leading genetic cause of kidney failure worldwide. It is characterized by cyst formation and growth, kidney parenchymal destruction, and complications including cyst infection, nephrolithiasis, cyst rupture, and cyst hemorrhage. Cyst bleeding is typically a self-limited event. This case report describes a 60-year-old man with ADPKD admitted with retroperitoneal hemorrhage following renal cyst rupture requiring embolization of a bleeding left lumbar artery and use of tranexamic acid. CASE REPORT A 60-year-old man with ADPKD presented with altered mental status. Labs noted hemoglobin of 4.7 g/dL. Abdominal imaging revealed polycystic kidneys and large left retroperitoneal hematoma. Angiogram demonstrated active bleeding from left L3 lumbar artery which was embolized. He was admitted to intensive care unit for hemorrhagic shock requiring multiple blood transfusions. Hemoglobin continued to downtrend despite blood products with repeat imaging demonstrating expanding retroperitoneal bleed. He underwent repeat angiogram and though there was no active bleeding, prophylactic embolization of left L1, L3, L4 lumbar and left renal capsular arteries were performed. Hemoglobin stabilized for next 3 days but continued to downtrend subsequently. Oral tranexamic acid was trialed with stabilization of the hemoglobin. CONCLUSIONS Life-threatening retroperitoneal hemorrhage following cyst rupture in the absence of major trauma or use of anti-coagulants, is a rare complication in ADPKD. Treatment involves resuscitation with blood products, management of shock, and interventional radiology-guided embolization. Tranexamic acid may be considered when the above measures fail. Nephrectomy may be indicated for refractory bleeding. This report highlights the diagnosis and management of massive cyst bleeding in ADPKD.
常染色体显性多囊肾病(ADPKD)是全球导致肾衰竭的主要遗传病因。其特征为囊肿形成和生长、肾实质破坏以及包括囊肿感染、肾结石、囊肿破裂和囊肿出血在内的并发症。囊肿出血通常是自限性的。本病例报告描述了一名 60 岁男性,因肾囊肿破裂导致腹膜后出血,需要栓塞左侧腰动脉出血和使用氨甲环酸。
一名 60 岁男性,患有 ADPKD,因精神状态改变就诊。实验室检查发现血红蛋白为 4.7 g/dL。腹部影像学检查显示多囊肾和巨大的左腹膜后血肿。血管造影显示左侧 L3 腰椎动脉有活跃性出血,予以栓塞。他因失血性休克收入重症监护病房,需要多次输血。尽管输注了血液制品,但血红蛋白仍持续下降,重复影像学检查显示腹膜后出血扩大。他接受了重复血管造影检查,虽然没有活跃性出血,但对左侧 L1、L3、L4 腰椎和左肾包膜动脉进行了预防性栓塞。接下来的 3 天血红蛋白稳定,但随后继续下降。口服氨甲环酸使血红蛋白稳定。
在没有重大创伤或使用抗凝剂的情况下,囊肿破裂后发生危及生命的腹膜后出血是 ADPKD 的罕见并发症。治疗包括通过输血制品进行复苏、休克管理和介入放射学引导下的栓塞。如果上述措施失败,可以考虑使用氨甲环酸。对于难治性出血,可能需要肾切除术。本报告强调了 ADPKD 中大量囊肿出血的诊断和管理。