Kuo Ming-Chung, Chuang Wen-Yu, Chang Hung, Lin Tung-Huei, Wu Jin-Hou, Lin Tung-Liang, Ou Che-Wei, Hung Yu-Shin, Huang Ting-Yu, Huang Ying-Jung, Wang Po-Nan, Shih Lee-Yung
Division of Hematology-Oncology, Chang Gung University, Taoyuan, Taiwan.
College of Medicine, Chang Gung University, Taoyuan, Taiwan.
Am J Clin Pathol. 2023 May 2;159(5):474-483. doi: 10.1093/ajcp/aqac173.
The clinical presentations of essential thrombocythemia (ET) may be quite similar to early/prefibrotic primary myelofibrosis (pre-PMF), especially in pre-PMF presenting with thrombocytosis (pre-PMF-T), but may be associated with a different outcome. It is very important to distinguish these two entities. The aim of this study was to address the clinical and prognostic relevance of distinguishing pre-PMF-T from ET.
All patients, including 258 with ET and 105 with pre-PMF-T, received JAK2V617F, MPL (exon 10), and CALR (exon 9) mutation analysis and allele burden measurement for JAK2V617F and CALR mutants.
Patients with pre-PMF-T had an older age and higher leukocyte and platelet counts but lower hemoglobin levels than patients with ET. Patients with pre-PMF-T had a shorter overall, leukemia-free, and thrombosis-free survival compared with patients with ET. Patients with ET had a higher rate of cerebral ischemic stroke, whereas patients with pre-PMF-T tended to have splanchnic vein thrombosis. The frequencies of JAK2V617F, CALR, and MPL mutations and CALR allele burden were no different, but JAK2V617F allele burden was significantly higher in pre-PMF-T. Patients with pre-PMF-T with the JAK2V617F mutation had an inferior overall survival and thrombosis-free survival, whereas the status of driver gene mutations did not influence the outcomes of patients with ET.
ET and pre-PMF-T were two distinct disease entities and exhibited different clinical phenotype, genotype, and outcomes.
原发性血小板增多症(ET)的临床表现可能与早期/纤维化前原发性骨髓纤维化(pre-PMF)非常相似,尤其是在表现为血小板增多的pre-PMF(pre-PMF-T)中,但可能与不同的预后相关。区分这两种疾病非常重要。本研究的目的是探讨区分pre-PMF-T与ET的临床及预后相关性。
所有患者,包括258例ET患者和105例pre-PMF-T患者,均接受JAK2V617F、MPL(第10外显子)和CALR(第9外显子)突变分析以及JAK2V617F和CALR突变体的等位基因负担测量。
与ET患者相比,pre-PMF-T患者年龄更大,白细胞和血小板计数更高,但血红蛋白水平更低。与ET患者相比,pre-PMF-T患者的总生存期、无白血病生存期和无血栓生存期更短。ET患者发生脑缺血性卒中的发生率更高,而pre-PMF-T患者倾向于发生内脏静脉血栓形成。JAK2V617F、CALR和MPL突变的频率以及CALR等位基因负担没有差异,但pre-PMF-T患者的JAK2V617F等位基因负担显著更高。携带JAK2V617F突变的pre-PMF-T患者总生存期和无血栓生存期较差,而驱动基因突变状态不影响ET患者的预后。
ET和pre-PMF-T是两种不同的疾病实体,具有不同的临床表型、基因型和预后。