Division of Hematology and Oncology, Department of Medicine, Medical College of Wisconsin, 8701 Watertown Plank Road, HRC 5860, Milwaukee, WI, 53226, USA.
Medical College of Wisconsin Cancer Center, Milwaukee, WI, USA.
J Hematol Oncol. 2023 Mar 10;16(1):21. doi: 10.1186/s13045-023-01418-4.
Despite mitochondrial DNA (mtDNA) mutations are common events in cancer, their global frequency and clinical impact have not been comprehensively characterized in patients with myelodysplastic neoplasia (also known as myelodysplastic syndromes, MDS). Here we performed whole-genome sequencing (WGS) on samples obtained before allogenic hematopoietic cell transplantation (allo-HCT) from 494 patients with MDS who were enrolled in the Center for International Blood and Marrow Transplant Research. We evaluated the impact of mtDNA mutations on transplantation outcomes, including overall survival (OS), relapse, relapse-free survival (RFS), and transplant-related mortality (TRM). A random survival forest algorithm was applied to evaluate the prognostic performance of models that include mtDNA mutations alone and combined with MDS- and HCT-related clinical factors. A total of 2666 mtDNA mutations were identified, including 411 potential pathogenic variants. We found that overall, an increased number of mtDNA mutations was associated with inferior transplantation outcomes. Mutations in several frequently mutated mtDNA genes (e.g., MT-CYB and MT-ND5) were identified as independent predictors of OS, RFS, relapse and/or TRM after allo-HCT. Integration of mtDNA mutations into the models based on the Revised International Prognostic Scores (IPSS-R) and clinical factors related to MDS and allo-HCT could capture more prognostic information and significantly improve the prognostic stratification efforts. Our study represents the first WGS effort in MDS receiving allo-HCT and shows that there may be clinical utility of mtDNA variants to predict allo-HCT outcomes in combination with more standard clinical parameters.
尽管线粒体 DNA(mtDNA)突变是癌症中的常见事件,但它们在骨髓增生异常肿瘤(也称为骨髓增生异常综合征,MDS)患者中的总体频率和临床影响尚未得到全面描述。在这里,我们对 494 名接受异基因造血细胞移植(allo-HCT)的 MDS 患者在 allo-HCT 前获得的样本进行了全基因组测序(WGS),这些患者均被纳入国际血液和骨髓移植研究中心。我们评估了 mtDNA 突变对移植结果的影响,包括总生存率(OS)、复发、无复发生存率(RFS)和移植相关死亡率(TRM)。随机生存森林算法被用于评估仅包含 mtDNA 突变和包含 MDS 和 HCT 相关临床因素的模型的预后性能。共鉴定出 2666 个 mtDNA 突变,包括 411 个潜在致病性变异。我们发现,总的来说,mtDNA 突变数量的增加与移植结果不良相关。几种经常发生突变的 mtDNA 基因(例如 MT-CYB 和 MT-ND5)的突变被鉴定为 allo-HCT 后 OS、RFS、复发和/或 TRM 的独立预测因子。将 mtDNA 突变整合到基于修订后的国际预后评分(IPSS-R)和与 MDS 及 allo-HCT 相关的临床因素的模型中,可以捕获更多的预后信息,并显著改善预后分层工作。我们的研究代表了接受 allo-HCT 的 MDS 患者的首次 WGS 研究,表明 mtDNA 变体与更标准的临床参数相结合,可能具有预测 allo-HCT 结果的临床应用价值。