Primary odontogenic keratocyst in the cheek muscles: Report of the 4th case in the world and review of peripheral OKC literature.

INTRODUCTION AND IMPORTANCE

Odontogenic keratocyst (OKC) is a developmental odontogenic cyst that usually can be seen within the jaw bones. The cyst arises from the remnants of odontogenic epithelial cells in the jaw bones. In rare cases the cyst can arise in the extraosseous tissues like the gingiva which is the most common site. However, other uncommon sites like oral mucosa and orofacial muscles have been reported.

CASE PRESENTATION

In this article we present a case report of 17-years-old male patient who visited the dentist complaining of a swelling in the right cheek for almost 2 years. He had no medical history with medications or genetic diseases. The mass was removed by the oral surgeon then subjected to histological examination; it was found to be an intramuscular odontogenic keratocyst.

CLINICAL DISCUSSION

Intramuscular odontogenic keratocyst is a rare cyst that can be seen in the orofacial muscle, and it can be difficult to diagnose when only clinical and radiographic features are based, and the definitive diagnosis is based on histological examination. The treatment is complete surgical excision.

CONCLUSIONS

39 cases were reported and achieved since 1971 until now, most of them presented in the gingiva and buccal mucosa and extremely rare within the muscles.