Abraham Ruth Elizabeth, Min Gan Lay, Pauzi Ahmad Luqman Bin Md, Salim Noor Hafizah Abdul, Ismail Iskasymar
Department of Medicine, Newcastle University Medicine Malaysia, Selangor, Malaysia.
Department of Medicine, Faculty of Medicine and Health Sciences, University Putra Malaysia, Selangor, Malaysia.
Turk J Emerg Med. 2023 Jan 9;23(3):191-194. doi: 10.4103/2452-2473.367398. eCollection 2023 Jul-Sep.
Respiratory myoclonus, also known as belly dancer's dyskinesia (BDD), is a rare manifestation of movement disorder characterized by repetitive choreiform involuntary movements involving the anterior abdominal muscles, the diaphragm, and other respiratory muscles. Currently, there is no definite pathophysiology that clearly explains this condition. A 25-year-old male with a known case of BDD presented with an exacerbation of involuntary and continuous writhing movements of the abdominal wall muscles associated with abdominal pain and shortness of breath over the past 2 days. Subsequently, he was intubated due to worsening respiratory distress a few days after his admission. He was then put on ultrasound-guided botulinum toxin A injections of 25 units over the left hemidiaphragm regularly. His symptoms markedly improved since then as the attacks had reduced to 5-6 monthly intervals. Administration of ultrasound-guided botulinum toxin A injections may help to control the exacerbation of BDD and might be an option for cases refractory to medical treatment and phrenic nerve ablation.
呼吸性肌阵挛,也称为肚皮舞者运动障碍(BDD),是一种罕见的运动障碍表现,其特征为涉及前腹壁肌肉、膈肌和其他呼吸肌的重复性舞蹈样不自主运动。目前,尚无明确的病理生理学能清楚解释这种情况。一名已知患有BDD的25岁男性,在过去2天出现腹壁肌肉不自主且持续的扭动运动加剧,并伴有腹痛和呼吸急促。随后,他在入院几天后因呼吸窘迫加重而插管。然后,他定期接受超声引导下在左半膈肌注射25单位肉毒杆菌毒素A。自那时起,他的症状明显改善,发作频率降至每月5 - 6次。超声引导下注射肉毒杆菌毒素A可能有助于控制BDD的加重,对于药物治疗和膈神经消融难治的病例可能是一种选择。