• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

骨髓增生异常肿瘤中缺失 7 和 7q 的基因组学:从致病元凶到潜在的合成致死治疗靶点。

Genomics of deletion 7 and 7q in myeloid neoplasm: from pathogenic culprits to potential synthetic lethal therapeutic targets.

机构信息

Department of Translational Hematology and Oncology Research, Taussig Cancer Institute, Cleveland Clinic Foundation, Cleveland, OH, USA.

Department of Hematology, National Hospital Organization Kyoto Medical Center, Kyoto, Japan.

出版信息

Leukemia. 2023 Oct;37(10):2082-2093. doi: 10.1038/s41375-023-02003-x. Epub 2023 Aug 26.

DOI:10.1038/s41375-023-02003-x
PMID:37634012
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC10539177/
Abstract

Complete or partial deletions of chromosome 7 (-7/del7q) belong to the most frequent chromosomal abnormalities in myeloid neoplasm (MN) and are associated with a poor prognosis. The disease biology of -7/del7q and the genes responsible for the leukemogenic properties have not been completely elucidated. Chromosomal deletions may create clonal vulnerabilities due to haploinsufficient (HI) genes contained in the deleted regions. Therefore, HI genes are potential targets of synthetic lethal strategies. Through the most comprehensive multimodal analysis of more than 600 -7/del7q MN samples, we elucidated the disease biology and qualified a list of most consistently deleted and HI genes. Among them, 27 potentially synthetic lethal target genes were identified with the following properties: (i) unaffected genes by hemizygous/homozygous LOF mutations; (ii) prenatal lethality in knockout mice; and (iii) vulnerability of leukemia cells by CRISPR and shRNA knockout screens. In -7/del7q cells, we also identified 26 up or down-regulated genes mapping on other chromosomes as downstream pathways or compensation mechanisms. Our findings shed light on the pathogenesis of -7/del7q MNs, while 27 potential synthetic lethal target genes and 26 differential expressed genes allow for a therapeutic window of -7/del7q.

摘要

7 号染色体完全或部分缺失(-7/del7q)属于骨髓性肿瘤(MN)中最常见的染色体异常之一,并与预后不良相关。-7/del7q 的疾病生物学和导致白血病的基因尚未完全阐明。由于缺失区域中包含的杂合不足(HI)基因,染色体缺失可能会产生克隆脆弱性。因此,HI 基因是合成致死策略的潜在靶点。通过对 600 多个 -7/del7q MN 样本进行最全面的多模态分析,我们阐明了疾病生物学,并确定了一组最一致缺失和 HI 基因的清单。其中,有 27 个潜在的合成致死靶基因具有以下特性:(i)不受杂合/纯合 LOF 突变影响的基因;(ii)在敲除小鼠中具有产前致死性;(iii)CRISPR 和 shRNA 敲除筛选使白血病细胞脆弱。在 -7/del7q 细胞中,我们还鉴定了 26 个映射到其他染色体上的上调或下调基因,作为下游途径或补偿机制。我们的发现揭示了 -7/del7q MN 的发病机制,而 27 个潜在的合成致死靶基因和 26 个差异表达基因为 -7/del7q 提供了治疗窗口。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/e72aa481f7f7/41375_2023_2003_Fig7_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/abec81e22537/41375_2023_2003_Fig1_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/c9cb92845bd2/41375_2023_2003_Fig2_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/e7f46b6bc566/41375_2023_2003_Fig3_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/8876d2a310ab/41375_2023_2003_Fig4_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/5e065af43791/41375_2023_2003_Fig5_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/c61cd5501892/41375_2023_2003_Fig6_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/e72aa481f7f7/41375_2023_2003_Fig7_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/abec81e22537/41375_2023_2003_Fig1_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/c9cb92845bd2/41375_2023_2003_Fig2_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/e7f46b6bc566/41375_2023_2003_Fig3_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/8876d2a310ab/41375_2023_2003_Fig4_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/5e065af43791/41375_2023_2003_Fig5_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/c61cd5501892/41375_2023_2003_Fig6_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/236b/10539177/e72aa481f7f7/41375_2023_2003_Fig7_HTML.jpg

相似文献

1
Genomics of deletion 7 and 7q in myeloid neoplasm: from pathogenic culprits to potential synthetic lethal therapeutic targets.骨髓增生异常肿瘤中缺失 7 和 7q 的基因组学:从致病元凶到潜在的合成致死治疗靶点。
Leukemia. 2023 Oct;37(10):2082-2093. doi: 10.1038/s41375-023-02003-x. Epub 2023 Aug 26.
2
Cytogenetic deletion maps of hematologic neoplasms: circumstantial evidence for tumor suppressor loci.血液系统肿瘤的细胞遗传学缺失图谱:肿瘤抑制基因座的间接证据
Genes Chromosomes Cancer. 1993 Dec;8(4):205-18. doi: 10.1002/gcc.2870080402.
3
Molecular Pathogenesis of MDS.骨髓增生异常综合征的分子发病机制
Hematology Am Soc Hematol Educ Program. 2005:156-60. doi: 10.1182/asheducation-2005.1.156.
4
Frequent deletions of JARID2 in leukemic transformation of chronic myeloid malignancies.慢性髓性恶性肿瘤白血病转化中 JARID2 的频繁缺失。
Am J Hematol. 2012 Mar;87(3):245-50. doi: 10.1002/ajh.22257. Epub 2011 Dec 21.
5
Cytogenetic and molecular delineation of a region of chromosome 7 commonly deleted in malignant myeloid diseases.恶性髓系疾病中常见缺失的7号染色体区域的细胞遗传学和分子定位
Blood. 1996 Sep 15;88(6):1930-5.
6
The significance of CUX1 and chromosome 7 in myeloid malignancies.CUX1 和 7 号染色体在髓系恶性肿瘤中的意义。
Curr Opin Hematol. 2022 Mar 1;29(2):92-102. doi: 10.1097/MOH.0000000000000699.
7
Chromosomal deletions in AML.急性髓系白血病中的染色体缺失
Cancer Treat Res. 2010;145:59-66. doi: 10.1007/978-0-387-69259-3_4.
8
CUX1 is a haploinsufficient tumor suppressor gene on chromosome 7 frequently inactivated in acute myeloid leukemia.CUX1 是 7 号染色体上的一个杂合性缺失肿瘤抑制基因,在急性髓系白血病中经常失活。
Blood. 2013 Feb 7;121(6):975-83. doi: 10.1182/blood-2012-04-426965. Epub 2012 Dec 3.
9
The enigma of monosomy 7.单体型 7 之谜。
Blood. 2018 Jun 28;131(26):2891-2898. doi: 10.1182/blood-2017-12-822262. Epub 2018 Apr 3.
10
Distinct clinical and biological implications of in myeloid neoplasms.在髓系肿瘤中 的独特临床和生物学意义。
Blood Adv. 2019 Jul 23;3(14):2164-2178. doi: 10.1182/bloodadvances.2018028423.

引用本文的文献

1
Genomic landscape and clonal architecture in pediatric myeloid neoplasms with chromosome 7 deletions.伴有7号染色体缺失的儿童髓系肿瘤的基因组图谱和克隆结构
Blood Neoplasia. 2025 Mar 10;2(2):100093. doi: 10.1016/j.bneo.2025.100093. eCollection 2025 May.
2
NAMPT haploinsufficiency is a collateral lethal therapeutic vulnerability in high-risk myeloid malignancies with inactivation.烟酰胺磷酸核糖转移酶(NAMPT)单倍体不足是高危髓系恶性肿瘤中一种伴随失活的致死性治疗脆弱性。
Blood Neoplasia. 2025 May 19;2(3):100119. doi: 10.1016/j.bneo.2025.100119. eCollection 2025 Aug.
3
Application of Optical Genome Mapping for the Diagnosis and Risk Stratification of Myeloid and Lymphoid Malignancies.

本文引用的文献

1
Significance of hereditary gene alterations for the pathogenesis of adult bone marrow failure versus myeloid neoplasia.遗传性基因改变对成人骨髓衰竭与髓系肿瘤发病机制的意义。
Leukemia. 2022 Dec;36(12):2827-2834. doi: 10.1038/s41375-022-01729-4. Epub 2022 Oct 20.
2
Pathophysiologic and clinical implications of molecular profiles resultant from deletion 5q.5q 缺失导致的分子谱的病理生理和临床意义。
EBioMedicine. 2022 Jun;80:104059. doi: 10.1016/j.ebiom.2022.104059. Epub 2022 May 23.
3
CRISPR screening in human hematopoietic stem and progenitor cells reveals an enrichment for tumor suppressor genes within chromosome 7 commonly deleted regions.
光学基因组图谱在髓系和淋巴系恶性肿瘤诊断及风险分层中的应用
Int J Mol Sci. 2025 Jun 16;26(12):5763. doi: 10.3390/ijms26125763.
4
Multiplex gene editing models of del(7q) reveal combined and loss drives clonal expansion and drug resistance.7号染色体长臂缺失(del(7q))的多重基因编辑模型揭示,联合缺失和功能丧失驱动克隆性扩增和耐药性。
Blood Neoplasia. 2025 Mar 3;2(2):100083. doi: 10.1016/j.bneo.2025.100083. eCollection 2025 May.
5
Mutation dynamics from diagnosis to relapse in acute myeloid leukemia with chromosomal 7 deletions.伴有7号染色体缺失的急性髓系白血病从诊断到复发的突变动态变化
Leuk Lymphoma. 2025 Jul;66(7):1221-1233. doi: 10.1080/10428194.2025.2477723. Epub 2025 Mar 31.
6
LUC7 proteins define two major classes of 5' splice sites in animals and plants.LUC7蛋白在动物和植物中定义了两类主要的5'剪接位点。
Nat Commun. 2025 Feb 20;16(1):1574. doi: 10.1038/s41467-025-56577-4.
7
Emergence and Cytogenetic Clonal Evolution of Chromosome 7 Abnormalities in Myeloid Malignancies: Investigating the Role of Telomere Dysfunction.髓系恶性肿瘤中7号染色体异常的出现及细胞遗传学克隆进化:探究端粒功能障碍的作用
Int J Mol Sci. 2025 Jan 29;26(3):1162. doi: 10.3390/ijms26031162.
8
Abnormalities in Chromosomes 5 and 7 in Myelodysplastic Syndrome and Acute Myeloid Leukemia.骨髓增生异常综合征和急性髓系白血病中5号和7号染色体的异常
Ann Lab Med. 2025 Mar 1;45(2):133-145. doi: 10.3343/alm.2024.0477. Epub 2025 Jan 8.
9
Genomic characterization of AML with aberrations of chromosome 7: a multinational cohort of 519 patients.具有 7 号染色体异常的 AML 的基因组特征:一个由 519 名患者组成的多国队列。
J Hematol Oncol. 2024 Aug 19;17(1):70. doi: 10.1186/s13045-024-01590-1.
10
Malignant progression of preleukemic disorders.白血病前期疾病的恶性进展。
Blood. 2024 May 30;143(22):2245-2255. doi: 10.1182/blood.2023020817.
CRISPR 筛选人类造血干细胞和祖细胞揭示了染色体 7 常见缺失区域内肿瘤抑制基因的富集。
Leukemia. 2022 May;36(5):1421-1425. doi: 10.1038/s41375-021-01491-z. Epub 2022 Jan 17.
4
Acute Myeloid Leukemia Case after Gene Therapy for Sickle Cell Disease.镰状细胞病基因治疗后发生的急性髓系白血病病例。
N Engl J Med. 2022 Jan 13;386(2):138-147. doi: 10.1056/NEJMoa2109167. Epub 2021 Dec 12.
5
Clinical evolution, genetic landscape and trajectories of clonal hematopoiesis in SAMD9/SAMD9L syndromes.SAMD9/SAMD9L 综合征中的临床演变、遗传图谱和克隆性造血轨迹。
Nat Med. 2021 Oct;27(10):1806-1817. doi: 10.1038/s41591-021-01511-6. Epub 2021 Oct 7.
6
Machine learning integrates genomic signatures for subclassification beyond primary and secondary acute myeloid leukemia.机器学习整合基因组特征,可实现急性髓系白血病的主次分类之外的亚分类。
Blood. 2021 Nov 11;138(19):1885-1895. doi: 10.1182/blood.2020010603.
7
What's new in the pathogenesis and treatment of therapy-related myeloid neoplasms.治疗相关髓系肿瘤发病机制和治疗的新进展。
Blood. 2021 Sep 2;138(9):749-757. doi: 10.1182/blood.2021010764.
8
Molecular landscape and clonal architecture of adult myelodysplastic/myeloproliferative neoplasms.成人骨髓增生异常/骨髓增殖性肿瘤的分子特征和克隆结构。
Blood. 2020 Oct 15;136(16):1851-1862. doi: 10.1182/blood.2019004229.
9
Impact of somatic mutations in myelodysplastic patients with isolated partial or total loss of chromosome 7.孤立性部分或全部 7 号染色体缺失的骨髓增生异常患者体细胞突变的影响。
Leukemia. 2020 Sep;34(9):2441-2450. doi: 10.1038/s41375-020-0728-x. Epub 2020 Feb 17.
10
Knockout Mouse Models Provide Insight into the Biological Functions of CRL1 Components.基因敲除小鼠模型为研究 CRL1 组件的生物学功能提供了线索。
Adv Exp Med Biol. 2020;1217:147-171. doi: 10.1007/978-981-15-1025-0_10.