Baldazzi Carmen, Bandini Lorenza, Robustelli Valentina, Patuelli Agnese, Venturi Claudia, Grassi Alessandra, Marzocchi Giulia, Ielpo Angela, Solli Vincenza, Bochicchio Maria Teresa, Paolini Stefania, Sartor Chiara, Zingarelli Federico, Curti Antonio, Ottaviani Emanuela, Testoni Nicoletta
IRCCS Azienda Ospedaliero-Universitaria di Bologna, Istituto di Ematologia "Seràgnoli", 40138 Bologna, Italy.
Dipartimento di Scienze Mediche e Chirurgiche, Università di Bologna, 40138 Bologna, Italy.
Int J Mol Sci. 2025 Jan 29;26(3):1162. doi: 10.3390/ijms26031162.
Monosomy 7 and deletion 7q are common chromosomal abnormalities in myeloid malignancies, and they are associated with a poor prognosis. The mechanism underlying their acquisition remains elusive. We identified a cohort of 24 patients exhibiting clones with different chromosome 7 abnormalities, such as deletion 7q, unstable derivatives (ring chromosomes or 'naked' centromeres), and monosomy 7. We designated this group as having cytogenetic clonal evolution of chromosome 7 abnormalities (CCE7). In some cases, CCE7 correlated with disease progression, suggesting that deletions or other derivatives involving the q-arm of chromosome 7 may arise early in the disease course. These abnormalities may be transient but can potentially evolve into monosomy 7. Within the CCE7 group, telomere loss or shortening may contribute to chromosomal instability and the emergence of unstable derivatives, as the chromosome 7 derivatives displayed loss or rearrangement of subtelomeric regions. Moreover, we identified variants in genes implicated in telomere biology disorders and observed specific genetic mutation profiles associated with different chromosome 7 abnormalities. These findings shed light on a potential mechanism leading to monosomy 7 through the evolution of chromosome 7q abnormalities. Identifying patients at risk of developing monosomy 7, based on the presence of unstable derivatives with telomere loss or a specific mutation profile, could potentially enhance patient management and guide the development of novel therapeutic strategies.
7号染色体单体和7q缺失是髓系恶性肿瘤中常见的染色体异常,且与预后不良相关。其获得的潜在机制仍不清楚。我们鉴定了一组24例患者,他们表现出具有不同7号染色体异常的克隆,如7q缺失、不稳定衍生物(环状染色体或“裸露”着丝粒)和7号染色体单体。我们将该组定义为具有7号染色体异常的细胞遗传学克隆进化(CCE7)。在某些情况下,CCE7与疾病进展相关,这表明涉及7号染色体q臂的缺失或其他衍生物可能在疾病进程早期出现。这些异常可能是短暂的,但可能会演变成7号染色体单体。在CCE7组中,端粒丢失或缩短可能导致染色体不稳定以及不稳定衍生物的出现,因为7号染色体衍生物显示出亚端粒区域的丢失或重排。此外,我们在与端粒生物学障碍相关的基因中鉴定出变异,并观察到与不同7号染色体异常相关的特定基因突变谱。这些发现揭示了一种通过7q染色体异常进化导致7号染色体单体的潜在机制。基于存在伴有端粒丢失的不稳定衍生物或特定突变谱来识别有发生7号染色体单体风险的患者,可能会改善患者管理并指导新治疗策略的开发。