Department of General Surgery, Amrita Institute of Medical Sciences, Kochi, Kerala, India.
Department of Gastrointestinal Surgery and Solid Organ Transplantation, Amrita Institute of Medical Sciences and Research Centre, Cochin, Kerala, India.
BMJ Case Rep. 2023 Sep 26;16(9):e254732. doi: 10.1136/bcr-2023-254732.
A young male presented with intermittent high-grade fever, asymmetric polyarthritis and erythematous, tender nodules over left shin for 2 months duration. He had a history of alcohol dependence with multiple episodes of acute pancreatitis. With polyarthritis progressing relentlessly, unresponsive to non-steroidal anti-inflammatory drugs and steroids, a provisional diagnosis of sarcoidosis was considered. Indeed, he was treated with azathioprine and rituximab with no effect. Biopsy of the skin nodule revealed subcutaneous fat necrosis, foam cells, deposition of eosinophilic amorphous material and calcification. Synovial fluid aspiration from the arthritic knee obtained purulent but surprisingly culture-negative material, rich in triglycerides. Abdominal CT confirmed chronic pancreatitis. Final diagnosis of pancreatitis, panniculitis and polyarthritis (PPP) syndrome was made. He underwent surgical pancreatic ductal drainage leading to complete remission of symptoms. PPP syndrome triad occurs due to leakage of pancreatic enzymes into systemic circulation and subsequent fat necrosis. Surgical drainage of pancreatic duct is often curative.
一位年轻男性出现间歇性高热、不对称性多关节炎和左小腿红斑、触痛结节,病程持续 2 个月。他有酒精依赖病史,曾多次发生急性胰腺炎。由于多关节炎持续进展,对非甾体抗炎药和类固醇治疗无反应,考虑诊断为结节病。实际上,他接受了硫唑嘌呤和利妥昔单抗治疗,但没有效果。皮肤结节活检显示皮下脂肪坏死、泡沫细胞、嗜酸性无定形物质沉积和钙化。关节炎膝关节滑液抽吸获得脓性但令人惊讶的无培养物材料,富含甘油三酯。腹部 CT 证实为慢性胰腺炎。最终诊断为胰腺炎、脂膜炎和多关节炎(PPP)综合征。他接受了胰腺导管引流手术,症状完全缓解。PPP 综合征三联征是由于胰腺酶漏入体循环和随后的脂肪坏死引起的。胰腺导管的手术引流通常是有效的。