Badiger Vaishnavi Ashok, Balan Suma, Madan Sumanth, Gogineni Kishore Sai, Shah Hitesh, Narayanan Dhanya Lakshmi
Department of Medical Genetics, Kasturba Medical College, Manipal, Manipal Academy of Higher Education, Manipal.
Department of Rheumatology and Clinical Immunology, Amrita Institute of Medical Sciences, Kochi.
Clin Dysmorphol. 2024 Jan 1;33(1):27-30. doi: 10.1097/MCD.0000000000000476. Epub 2023 Oct 12.
LPIN2 -related Majeed syndrome (MIM# 609628) is a rare non-inflammasome autoinflammatory disease, caused due to biallelic variants in LPIN2 (MIM* 605519). To date, only 31 individuals from 18 families have been reported with this rare condition. Exome sequencing was done in two affected individuals from two unrelated families. Additionally, phenotypic, and genotypic information from the literature was reviewed. Two novel homozygous missense variants, c.2207G>A p. (Arg736His) and c.1157C>G p. (Ser386Ter) in LPIN2 , were identified in family 1 and family 2 respectively. Chronic recurrent osteomyelitis involving the lower extremities was the most common clinical presentation. LPIN2 -related Majeed syndrome should be considered as a differential diagnosis in an individual with clinical or radiological evidence of recurrent sterile osteomyelitis and chronic anaemia.
与LPIN2相关的马吉德综合征(MIM# 609628)是一种罕见的非炎性小体自身炎症性疾病,由LPIN2基因(MIM* 605519)的双等位基因变异引起。迄今为止,仅报道了来自18个家庭的31例个体患有这种罕见疾病。对来自两个无关家庭的两名患病个体进行了外显子组测序。此外,还回顾了文献中的表型和基因型信息。分别在家庭1和家庭2中鉴定出LPIN2基因的两个新的纯合错义变异,即c.2207G>A p.(Arg736His)和c.1157C>G p.(Ser386Ter)。累及下肢的慢性复发性骨髓炎是最常见的临床表现。对于有复发性无菌性骨髓炎和慢性贫血的临床或影像学证据的个体,应考虑将与LPIN2相关的马吉德综合征作为鉴别诊断。