• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

一名成年患者因儿童期诊断为威尔逊-米基蒂综合征而接受气胸手术切除。

Surgical Resection of a Pneumothorax in an Adult Patient With a History of Wilson-Mikity Syndrome Diagnosed in Childhood.

作者信息

Yoshino Ryusei, Nakatsubo Masaki, Ujiie Nanami, Kitada Masahiro

机构信息

Thoracic Surgery and Breast Surgery, Asahikawa Medical University Hospital, Asahikawa, JPN.

出版信息

Cureus. 2024 Feb 21;16(2):e54641. doi: 10.7759/cureus.54641. eCollection 2024 Feb.

DOI:10.7759/cureus.54641
PMID:38523925
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC10960230/
Abstract

Wilson-Mikity syndrome (WMS) is a rare condition characterized by various respiratory and pulmonary abnormalities in neonates and infants. However, the diagnosis is based on the findings of physiological tests, such as respiratory function tests. Reports describing the histopathological features of WMS are limited. The patient was a 22-year-old woman with a history of WMS. She had been on a ventilator for the first three months of life due to pulmonary hypertension after early delivery at 24 weeks of gestation and required oxygen therapy until three years of age. One month before presenting at our clinic, the patient experienced chest pain and respiratory distress, and a left spontaneous pneumothorax was diagnosed based on a chest X-ray examination. The pneumothorax improved after the insertion of a thoracic drain but recurred soon thereafter. A histopathological examination revealed emphysematous changes associated with WMS in the background lungs, consistent with brevity. No postoperative complications were observed. The thoracic drain was removed on the second day, and the patient was discharged on the eighth postoperative day. Postoperatively, the patient was started on inhaled medication and was carefully monitored every three months. The present case suggests that childhood interviews are very important for adult patients who develop pneumothorax and that early surgical treatment may be selected based on a detailed interview. Moreover, postoperative follow-up should be carefully performed in collaboration with respiratory medicine in patients with pneumothorax originating from chronic obstructive pulmonary diseases such as WMS.

摘要

威尔逊-米基蒂综合征(WMS)是一种罕见病症,其特征为新生儿和婴儿出现各种呼吸及肺部异常。然而,诊断基于生理测试结果,如呼吸功能测试。描述WMS组织病理学特征的报告有限。该患者为一名22岁女性,有WMS病史。她在妊娠24周早产出生后,因肺动脉高压在出生后的头三个月使用呼吸机,并且在三岁前一直需要吸氧治疗。在到我们诊所就诊前一个月,患者出现胸痛和呼吸窘迫,胸部X线检查诊断为左侧自发性气胸。胸腔引流管置入后气胸有所改善,但随后很快复发。组织病理学检查显示,背景肺组织存在与WMS相关的肺气肿改变,与简述一致。未观察到术后并发症。术后第二天拔除胸腔引流管,患者在术后第八天出院。术后,患者开始吸入药物治疗,并每三个月接受仔细监测。本病例表明,对于发生气胸的成年患者,儿童时期的问诊非常重要,并且可以根据详细问诊选择早期手术治疗。此外,对于源自慢性阻塞性肺疾病如WMS的气胸患者,术后应与呼吸内科合作仔细进行随访。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/cf31753eba5a/cureus-0016-00000054641-i04.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/8c94900f09ff/cureus-0016-00000054641-i01.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/c75dd0793cdc/cureus-0016-00000054641-i02.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/b63d05fa1e68/cureus-0016-00000054641-i03.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/cf31753eba5a/cureus-0016-00000054641-i04.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/8c94900f09ff/cureus-0016-00000054641-i01.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/c75dd0793cdc/cureus-0016-00000054641-i02.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/b63d05fa1e68/cureus-0016-00000054641-i03.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/7a36/10960230/cf31753eba5a/cureus-0016-00000054641-i04.jpg

相似文献

1
Surgical Resection of a Pneumothorax in an Adult Patient With a History of Wilson-Mikity Syndrome Diagnosed in Childhood.一名成年患者因儿童期诊断为威尔逊-米基蒂综合征而接受气胸手术切除。
Cureus. 2024 Feb 21;16(2):e54641. doi: 10.7759/cureus.54641. eCollection 2024 Feb.
2
Bubbly and cystic appearance in chronic lung disease: Is this diagnosed as Wilson-Mikity syndrome?慢性肺病中的气泡样和囊状表现:这能被诊断为威尔逊-米基蒂综合征吗?
Pediatr Int. 2016 Apr;58(4):251-3. doi: 10.1111/ped.12901. Epub 2016 Mar 7.
3
[Standard technical specifications for methacholine chloride (Methacholine) bronchial challenge test (2023)].[氯化乙酰甲胆碱支气管激发试验标准技术规范(2023年)]
Zhonghua Jie He He Hu Xi Za Zhi. 2024 Feb 12;47(2):101-119. doi: 10.3760/cma.j.cn112147-20231019-00247.
4
Cytomegalovirus associated neonatal pneumonia and Wilson-Mikity syndrome: a causal relationship?巨细胞病毒相关的新生儿肺炎与威尔逊-米基蒂综合征:存在因果关系吗?
Eur Respir J. 1999 Feb;13(2):460-2. doi: 10.1183/09031936.99.13246099.
5
Chronic lung disease in extremely low birth weight infants: a two-year retrospective analysis.极低出生体重儿慢性肺部疾病:一项为期两年的回顾性分析。
Acta Paediatr Taiwan. 2000 Mar-Apr;41(2):75-9.
6
High-resolution CT findings in Wilson-Mikity syndrome: a case report.威尔逊-米基蒂综合征的高分辨率CT表现:一例报告
Pediatr Radiol. 1998 Sep;28(9):691-3. doi: 10.1007/s002470050441.
7
[Chinese experts consensus statement: diagnosis and treatment of cystic fibrosis (2023)].[中国专家共识声明:囊性纤维化的诊断与治疗(2023年)]
Zhonghua Jie He He Hu Xi Za Zhi. 2023 Apr 12;46(4):352-372. doi: 10.3760/cma.j.cn112147-20221214-00971.
8
Wilson-Mikity syndrome: updated diagnostic criteria based on nine cases and a review of the literature.威尔逊-米基蒂综合征:基于9例病例及文献综述的更新诊断标准
Pediatr Pulmonol. 2008 Oct;43(10):1004-12. doi: 10.1002/ppul.20900.
9
An early case of pulmonary lymphangioleiomyomatosis diagnosed by video-assisted thoracoscopic surgery.一例通过电视辅助胸腔镜手术诊断的肺淋巴管平滑肌瘤病早期病例。
Ann Thorac Cardiovasc Surg. 2005 Dec;11(6):405-7.
10
Abnormal pulmonary bombesin immunoreactive cells in Wilson-Mikity syndrome (pulmonary dysmaturity) and bronchopulmonary dysplasia.威尔逊-米基蒂综合征(肺发育不全)和支气管肺发育不良中异常的肺蛙皮素免疫反应性细胞。
Pediatr Pathol. 1993 Mar-Apr;13(2):165-80. doi: 10.3109/15513819309048204.

本文引用的文献

1
A Case of Pneumothorax Ex Vacuo Associated with COVID-19.一例与 COVID-19 相关的气胸(ex vacuo)。
Medicina (Kaunas). 2023 Apr 4;59(4):709. doi: 10.3390/medicina59040709.
2
Perinatal Nutritional and Metabolic Pathways: Early Origins of Chronic Lung Diseases.围产期营养与代谢途径:慢性肺部疾病的早期起源
Front Med (Lausanne). 2021 Jun 15;8:667315. doi: 10.3389/fmed.2021.667315. eCollection 2021.
3
Pulmonary Hypertension.肺动脉高压
Ann Intern Med. 2021 Apr;174(4):ITC49-ITC64. doi: 10.7326/AITC202104200. Epub 2021 Apr 13.
4
Histological chorioamnionitis and its impact on respiratory outcome in very-low-birth-weight preterm infants.组织学绒毛膜羊膜炎及其对极低出生体重早产儿呼吸结局的影响。
Pediatr Neonatol. 2021 May;62(3):258-264. doi: 10.1016/j.pedneo.2020.11.009. Epub 2021 Jan 20.
5
50 Years Ago in The Journal of Pediatrics: Wilson-Mikity Syndrome.50年前《儿科学杂志》刊载:威尔逊-米基蒂综合征。
J Pediatr. 2020 Jul;222:173. doi: 10.1016/j.jpeds.2020.01.037.
6
Early-onset chronic obstructive pulmonary disease in Wilson-Mikity syndrome with preterm birth.Wilson-Mikity综合征合并早产患儿的早发型慢性阻塞性肺疾病
Pediatr Int. 2017 Mar;59(3):364-365. doi: 10.1111/ped.13205.
7
From Wilson and Mikity to Hyde.从威尔逊和米基蒂到海德。
Arch Argent Pediatr. 2016 Feb;114(1):96. doi: 10.5546/aap.2016.eng.96.
8
Bubbly and cystic appearance in chronic lung disease: Is this diagnosed as Wilson-Mikity syndrome?慢性肺病中的气泡样和囊状表现:这能被诊断为威尔逊-米基蒂综合征吗?
Pediatr Int. 2016 Apr;58(4):251-3. doi: 10.1111/ped.12901. Epub 2016 Mar 7.
9
Pulmonary hypertension in chronic lung disease of infancy.婴儿期慢性肺部疾病中的肺动脉高压
Curr Opin Pediatr. 2015 Apr;27(2):177-83. doi: 10.1097/MOP.0000000000000205.