Department of Neuroscience, Baylor College of Medicine, Houston, TX 77030, USA.
Department of Pathology and Immunology, Baylor College of Medicine, Houston, TX 77030, USA.
Dis Model Mech. 2024 Jun 1;17(6). doi: 10.1242/dmm.050379. Epub 2024 Jun 12.
Purkinje cell dysfunction disrupts movement and causes disorders such as ataxia. Recent evidence suggests that Purkinje cell dysfunction may also alter sleep regulation. Here, we used an ataxic mouse model generated by silencing Purkinje cell neurotransmission (L7Cre;Vgatfx/fx) to better understand how cerebellar dysfunction impacts sleep physiology. We focused our analysis on sleep architecture and electrocorticography (ECoG) patterns based on their relevance to extracting physiological measurements during sleep. We found that circadian activity was unaltered in the mutant mice, although their sleep parameters and ECoG patterns were modified. The L7Cre;Vgatfx/fx mutant mice had decreased wakefulness and rapid eye movement (REM) sleep, whereas non-REM sleep was increased. The mutants had an extended latency to REM sleep, which is also observed in human patients with ataxia. Spectral analysis of ECoG signals revealed alterations in the power distribution across different frequency bands defining sleep. Therefore, Purkinje cell dysfunction may influence wakefulness and equilibrium of distinct sleep stages in ataxia. Our findings posit a connection between cerebellar dysfunction and disrupted sleep and underscore the importance of examining cerebellar circuit function in sleep disorders.
浦肯野细胞功能障碍会扰乱运动,并导致共济失调等疾病。最近的证据表明,浦肯野细胞功能障碍也可能改变睡眠调节。在这里,我们使用沉默浦肯野细胞神经传递(L7Cre; Vgatfx/fx)的共济失调小鼠模型来更好地了解小脑功能障碍如何影响睡眠生理。我们的分析集中在睡眠结构和脑电图(ECoG)模式上,因为它们与在睡眠期间提取生理测量值有关。我们发现,突变小鼠的昼夜活动没有改变,尽管它们的睡眠参数和 ECoG 模式发生了改变。L7Cre; Vgatfx/fx 突变小鼠的觉醒和快速眼动(REM)睡眠减少,而非 REM 睡眠增加。突变体的 REM 睡眠潜伏期延长,这在共济失调的人类患者中也观察到。ECoG 信号的频谱分析显示,不同频率带定义的睡眠的功率分布发生了改变。因此,浦肯野细胞功能障碍可能会影响共济失调患者不同睡眠阶段的觉醒和平衡。我们的研究结果表明小脑功能障碍与睡眠中断之间存在联系,并强调了在睡眠障碍中检查小脑回路功能的重要性。