Fontecha María Belén, Anadón María Del Rosario, Mercado Guzmán Verónica, Stanganelli Carmen, Galvano Camila, Tosin Fernanda, Bordone Javier, Bezares Raimundo, Rodríguez Cecilia, Heller Viviana, Slavutsky Irma, Fundia Ariela Freya
Laboratorio de Farmacogenómica, Instituto de Medicina Experimental, CONICET-Academia Nacional de Medicina, Buenos Aires, Argentina.
Laboratorio de Biología Molecular, Hospital Alemán, Buenos Aires, Argentina.
Ann Hematol. 2024 Dec;103(12):5703-5712. doi: 10.1007/s00277-024-05794-w. Epub 2024 May 14.
TP53 gene disruption, including 17p13 deletion [del(17p)] and/or TP53 mutations, is a negative prognostic biomarker in chronic lymphocytic leukemia (CLL) associated with disease progression, treatment failure and shorter survival. Germline variants in p53 signaling pathway genes could also lead to p53 dysfunction, but their involvement in CLL has not been thoroughly evaluated. The aim of this study was to determine the association of TP53, MDM2 and NQO1 gene variability with clinical and genetic data of CLL patients. Individual genotype and haplotype data of CLL patients were compared with clinical prognostic factors, cytogenetic and molecular cytogenetic findings as well as IGHV and TP53 mutational status. The study included 116 CLL patients and 161 healthy blood donors. TP53 (rs1042522, rs59758982, rs1625895), NQO1 (rs1800566) and MDM2 (rs2279744, rs150550023) variants were genotyped using different PCR approaches. Analysis of genotype frequencies revealed no association with the risk of CLL. TP53 rs1042522, rs1625895 and MDM2 rs2279744 variants were significantly associated with abnormal karyotype and the presence of del(17p). Similarly, these two TP53 variants were associated with TP53 disruption. Moreover, TP53 C-A-nondel and G-A-del haplotypes (rs1042522-rs1625895-rs59758982) were associated with an increased likelihood of carrying del(17p) and TP53 disruptions. MDM2 T-nondel haplotype (rs2279744-rs150550023) was found to be a low risk factor for del(17p) (OR = 0.32; CI: 0.12-0.82; p = 0.02) and TP53 disruptions (OR = 0.41; CI: 0.18-0.95; p = 0.04). Our findings suggest that TP53 and MDM2 variants may modulate the risk to have chromosome alterations and TP53 disruptions, particularly del(17p). To our knowledge this is the first study of several germline variants in p53 pathway genes in Argentine patients with CLL.
TP53基因破坏,包括17p13缺失[del(17p)]和/或TP53突变,是慢性淋巴细胞白血病(CLL)中的一种不良预后生物标志物,与疾病进展、治疗失败和较短生存期相关。p53信号通路基因中的种系变异也可能导致p53功能障碍,但其在CLL中的作用尚未得到充分评估。本研究的目的是确定TP53、MDM2和NQO1基因变异与CLL患者临床和遗传数据之间的关联。将CLL患者的个体基因型和单倍型数据与临床预后因素、细胞遗传学和分子细胞遗传学结果以及IGHV和TP53突变状态进行比较。该研究纳入了116例CLL患者和161名健康献血者。使用不同的PCR方法对TP53(rs1042522、rs59758982、rs1625895)、NQO1(rs1800566)和MDM2(rs2279744、rs150550023)变异进行基因分型。基因型频率分析显示与CLL风险无关联。TP53 rs1042522、rs1625895和MDM2 rs2279744变异与异常核型和del(17p)的存在显著相关。同样,这两个TP53变异与TP53破坏相关。此外,TP53 C-A-非缺失和G-A-缺失单倍型(rs1042522-rs1625895-rs59758982)与携带del(17p)和TP53破坏的可能性增加相关。发现MDM2 T-非缺失单倍型(rs2279744-rs150550023)是del(17p)(OR = 0.32;CI:0.12 - 0.82;p = 0.02)和TP53破坏(OR = 0.41;CI:0.18 - 0.95;p = 0.04)的低风险因素。我们的研究结果表明,TP53和MDM2变异可能调节发生染色体改变和TP53破坏的风险,尤其是del(17p)。据我们所知,这是对阿根廷CLL患者p53通路基因中几种种系变异的首次研究。