Department of Radiation Oncology, University of Michigan, Ann Arbor, Michigan.
Department of Internal Medicine, University of Michigan, Ann Arbor, Michigan.
Mol Cancer Res. 2024 Nov 1;22(11):996-1010. doi: 10.1158/1541-7786.MCR-24-0361.
Frequent (>70%) TP53 mutations often promote its protein stabilization, driving esophageal adenocarcinoma (EAC) development linked to poor survival and therapy resistance. We previously reported that during Barrett's esophagus progression to EAC, an isoform switch occurs in the E3 ubiquitin ligase RNF128 (aka GRAIL-gene related to anergy in lymphocytes), enriching isoform 1 (hereby GRAIL1) and stabilizing the mutant p53 protein. Consequently, GRAIL1 knockdown degrades mutant p53. But, how GRAIL1 stabilizes the mutant p53 protein remains unclear. In search for a mechanism, here, we performed biochemical and cell biology studies to identify that GRAIL has a binding domain (315-PMCKCDILKA-325) for heat shock protein 40/DNAJ. This interaction can influence DNAJ chaperone activity to modulate misfolded mutant p53 stability. As predicted, either the overexpression of a GRAIL fragment (Frag-J) encompassing the DNAJ binding domain or a cell-permeable peptide (Pep-J) encoding the above 10 amino acids can bind and inhibit DNAJ-Hsp70 co-chaperone activity, thus degrading misfolded mutant p53. Consequently, either Frag-J or Pep-J can reduce the survival of mutant p53 containing dysplastic Barrett's esophagus and EAC cells and inhibit the growth of patient-derived organoids of dysplastic Barrett's esophagus in 3D cultures. The misfolded mutant p53 targeting and growth inhibitory effects of Pep-J are comparable with simvastatin, a cholesterol-lowering drug that can degrade misfolded mutant p53 also via inhibiting DNAJA1, although by a distinct mechanism. Implications: We identified a novel ubiquitin ligase-independent, chaperone-regulating domain in GRAIL and further synthesized a first-in-class novel misfolded mutant p53 degrading peptide having future translational potential.
频繁 (>70%) 的 TP53 突变常促进其蛋白稳定,导致与不良预后和治疗抵抗相关的食管腺癌 (EAC) 发生。我们之前报道,在 Barrett 食管进展为 EAC 的过程中,E3 泛素连接酶 RNF128(又名 GRAIL-与淋巴细胞无反应性相关的基因)的异构体发生转换,富集异构体 1(即 GRAIL1)并稳定突变型 p53 蛋白。因此,GRAIL1 的敲低会降解突变型 p53。但是,GRAIL1 如何稳定突变型 p53 蛋白尚不清楚。为了寻找机制,我们在此进行了生化和细胞生物学研究,以确定 GRAIL 具有与热休克蛋白 40/DNAJ 结合的结构域(315-PMCKCDILKA-325)。这种相互作用可以影响 DNAJ 伴侣蛋白的活性,从而调节错误折叠的突变型 p53 的稳定性。正如所预测的,包含 DNAJ 结合结构域的 GRAIL 片段(Frag-J)或编码上述 10 个氨基酸的细胞穿透肽(Pep-J)的过表达可以结合并抑制 DNAJ-Hsp70 共伴侣活性,从而降解错误折叠的突变型 p53。因此,Frag-J 或 Pep-J 均可降低含异型增生 Barrett 食管和 EAC 细胞的突变型 p53 的存活,并抑制 3D 培养中异型增生 Barrett 食管患者来源类器官的生长。Pep-J 对错误折叠的突变型 p53 的靶向和生长抑制作用与辛伐他汀相当,辛伐他汀是一种降低胆固醇的药物,也可以通过抑制 DNAJA1 降解错误折叠的突变型 p53,尽管作用机制不同。意义:我们在 GRAIL 中鉴定了一个新的泛素连接酶非依赖、伴侣调节结构域,并进一步合成了首个具有未来转化潜力的新型错误折叠的突变型 p53 降解肽。