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孤立性结膜海绵状血管瘤:一例罕见病例报告。

Isolated conjunctival cavernous hemangioma: a rare case report.

机构信息

Tavallali Eye Infirmary, Shiraz, Iran.

Student Research Committee, Kermanshah University of Medical Sciences, Kermanshah, Iran.

出版信息

BMC Ophthalmol. 2024 Jul 25;24(1):311. doi: 10.1186/s12886-024-03572-w.

DOI:10.1186/s12886-024-03572-w
PMID:39054506
原文链接:https://pmc.ncbi.nlm.nih.gov/articles/PMC11274753/
Abstract

Vascular conjunctival tumors are uncommon, usually benign lesions. Here, we report a 65-year-old male who presented with a nasal interpalpebral bulbar firm, oval, and dark-brown and non-mobile conjunctival mass. The systemic and ocular examinations including fundoscopy and gonioscopy were within normal limits. With a diagnosis of conjunctival malignant melanoma (CMM), the patient underwent excisional biopsy, partial sclerectomy, and cryotherapy. Microscopic examination revealed dilated vascular channels filled by red blood cells, separated by fibrous interstitium and no sign of malignancy. Therefore, a diagnosis of conjunctival cavernous hemangioma was made. Our case demonstrates that the conjunctival cavernous hemangioma can mimic malignant conjunctival lesions as well as extrascleral extension of uveal melanoma or uveal prolapse due to scleral necrosis.

摘要

血管性结膜肿瘤并不常见,通常为良性病变。在此,我们报告了 1 例 65 岁男性,其表现为鼻侧球结膜处质硬、椭圆形、暗棕色、不可移动的结膜肿块。全身和眼部检查,包括眼底镜和房角镜检查均未见异常。诊断为结膜恶性黑色素瘤(CMM),患者接受了切除术、部分巩膜切除术和冷冻疗法。显微镜检查显示,扩张的血管通道充满红细胞,纤维间质分隔,无恶性征象。因此,诊断为结膜海绵状血管瘤。我们的病例表明,结膜海绵状血管瘤可模拟恶性结膜病变以及葡萄膜黑色素瘤或葡萄膜脱出的巩膜坏死性 extrascleral 延伸。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/2d49384ae511/12886_2024_3572_Fig4_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/48589cc48701/12886_2024_3572_Fig1_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/391192036087/12886_2024_3572_Fig2_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/990a6e20958b/12886_2024_3572_Fig3_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/2d49384ae511/12886_2024_3572_Fig4_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/48589cc48701/12886_2024_3572_Fig1_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/391192036087/12886_2024_3572_Fig2_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/990a6e20958b/12886_2024_3572_Fig3_HTML.jpg
https://cdn.ncbi.nlm.nih.gov/pmc/blobs/d4dc/11274753/2d49384ae511/12886_2024_3572_Fig4_HTML.jpg

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本文引用的文献

1
Large benign de novo conjunctival hemangioma in an 11-year-old boy: case report and literature review.一名11岁男孩的大型原发性良性结膜血管瘤:病例报告及文献综述
J AAPOS. 2016 Oct;20(5):462-464. doi: 10.1016/j.jaapos.2016.06.002. Epub 2016 Sep 16.
2
Management of conjunctival malignant melanoma: a review and update.结膜恶性黑色素瘤的管理:综述与更新
Expert Rev Ophthalmol. 2014 Jun;9(3):185-204. doi: 10.1586/17469899.2014.921119.
3
Vascular tumors of the conjunctiva in 140 cases.结膜血管肿瘤 140 例。
Ophthalmology. 2011 Sep;118(9):1747-53. doi: 10.1016/j.ophtha.2011.04.034. Epub 2011 Jul 23.