Goncalves Maria B, Wu Yue, Clarke Earl, Grist John, Moehlin Julien, Mendoza-Parra Marco Antonio, Hobbs Carl, Kalindjian Barret, Fok Henry, Mander Adrian P, Hassanin Hana, Bendel Daryl, Täubel Jörg, Mant Tim, Carlstedt Thomas, Jack Julian, Corcoran Jonathan P T
Neuroscience Drug Discovery Unit, Wolfson Sensory, Pain and Regeneration Centre, King's College London, Guy's Campus, London, United Kingdom.
UMR 8030 Génomique Métabolique, Genoscope, Institut François Jacob, CEA, CNRS, University of Évry-val-d'Essonne, University Paris-Saclay, Évry, France.
Front Mol Neurosci. 2024 Aug 20;17:1411384. doi: 10.3389/fnmol.2024.1411384. eCollection 2024.
Retinoic acid receptor β2 (RARβ2) is an emerging therapeutic target for spinal cord injuries (SCIs) with a unique multimodal regenerative effect. We have developed a first-in-class RARβ agonist drug, C286, that modulates neuron-glial pathways to induce functional recovery in a rodent model of sensory root avulsion. Here, using genome-wide and pathway enrichment analysis of avulsed rats' spinal cords, we show that C286 also influences the extracellular milieu (ECM). Protein expression studies showed that C286 upregulates tenascin-C, integrin-α9, and osteopontin in the injured cord. Similarly, C286 remodulates these ECM molecules, hampers inflammation and prevents tissue loss in a rodent model of spinal cord contusion C286. We further demonstrate C286's efficacy in human iPSC-derived neurons, with treatment resulting in a significant increase in neurite outgrowth. Additionally, we identify a putative efficacy biomarker, S100B, which plasma levels correlated with axonal regeneration in nerve-injured rats. We also found that other clinically available retinoids, that are not RARβ specific agonists, did not lead to functional recovery in avulsed rats, demonstrating the requirement for RARβ specific pathways in regeneration. In a Phase 1 trial, the single ascending dose (SAD) cohorts showed increases in expression of RARβ2 in white blood cells correlative to increased doses and at the highest dose administered, the pharmacokinetics were similar to the rat proof of concept (POC) studies. Collectively, our data suggests that C286 signalling in neurite/axonal outgrowth is conserved between species and across nerve injuries. This warrants further clinical testing of C286 to ascertain POC in a broad spectrum of neurodegenerative conditions.
维甲酸受体β2(RARβ2)是脊髓损伤(SCI)新出现的治疗靶点,具有独特的多模式再生效应。我们已研发出同类首创的RARβ激动剂药物C286,其可调节神经元-胶质细胞通路,在感觉根撕脱伤的啮齿动物模型中诱导功能恢复。在此,通过对撕脱伤大鼠脊髓进行全基因组和通路富集分析,我们发现C286还会影响细胞外环境(ECM)。蛋白质表达研究表明,C286可上调损伤脊髓中的腱生蛋白-C、整合素-α9和骨桥蛋白。同样,在脊髓挫伤的啮齿动物模型C286中,C286可重塑这些ECM分子,抑制炎症并防止组织损失。我们进一步证明了C286对人诱导多能干细胞衍生神经元的疗效,治疗后神经突生长显著增加。此外,我们确定了一个假定的疗效生物标志物S100B,其血浆水平与神经损伤大鼠的轴突再生相关。我们还发现,其他临床上可用的非RARβ特异性激动剂类视黄醇不会导致撕脱伤大鼠功能恢复,这表明再生过程中需要RARβ特异性通路。在1期试验中,单次递增剂量(SAD)队列显示白细胞中RARβ2的表达随剂量增加而升高,在最高给药剂量下,药代动力学与大鼠概念验证(POC)研究相似。总体而言,我们的数据表明,C286在神经突/轴突生长中的信号传导在不同物种间以及不同神经损伤中具有保守性。这使得有必要对C286进行进一步的临床试验,以确定其在广泛的神经退行性疾病中的概念验证。