Hamdan Ahmad, Chou Chun, Rust Daniel, Strand Andrew
Infectious Diseases, Tufts Medical Center, Boston, USA.
Internal Medicine, University of Pennsylvania, Philadelphia, USA.
Cureus. 2024 Aug 6;16(8):e66338. doi: 10.7759/cureus.66338. eCollection 2024 Aug.
A 24-year-old Ecuadorian female, previously diagnosed with acute fatty liver (AFL) during pregnancy, developed constitutional symptoms, jaundice, and abdominal pain in a subsequent pregnancy, prompting investigations that suggested a recurrence of AFL. She underwent an elective abortion, which resulted in the resolution of her abdominal pain, and a liver biopsy, which showed granulomatous inflammation and lymphocytic infiltration. She later presented with abdominal distention, productive cough, and persistent constitutional symptoms and jaundice. Extensive laboratory and imaging studies indicated sepsis, acute liver injury, and disseminated intravascular coagulopathy. Her serum Epstein-Barr virus (EBV) level was elevated. Special staining of her previous liver biopsy revealed EBV-positive natural killer (NK) cells. A bone marrow biopsy also revealed EBV-positive NK cells. She was diagnosed with aggressive NK cell leukemia (ANKL) with or without chronic active EBV (CAEBV). Treatment included dexamethasone, atovaquone, bortezomib, and ganciclovir, with plans for a stem cell transplant. However, her course was complicated by infections and multi-organ failure, resulting in her passing. This case highlights the rarity and challenges in managing EBV-associated ANKL, emphasizing the need for early detection and improved treatment options, with stem cell transplantation offering the best prognosis.
一名24岁的厄瓜多尔女性,曾在孕期被诊断为急性脂肪肝(AFL),在随后的一次怀孕中出现全身症状、黄疸和腹痛,促使相关检查提示AFL复发。她接受了选择性流产,腹痛得以缓解,并进行了肝脏活检,结果显示为肉芽肿性炎症和淋巴细胞浸润。她后来出现腹胀、咳痰,持续存在全身症状和黄疸。广泛的实验室检查和影像学研究表明存在脓毒症、急性肝损伤和弥散性血管内凝血。她的血清爱泼斯坦-巴尔病毒(EBV)水平升高。对其之前肝脏活检的特殊染色显示EBV阳性自然杀伤(NK)细胞。骨髓活检也显示EBV阳性NK细胞。她被诊断为侵袭性NK细胞白血病(ANKL),伴或不伴慢性活动性EBV(CAEBV)。治疗包括地塞米松、阿托伐醌、硼替佐米和更昔洛韦,并计划进行干细胞移植。然而,她的病程因感染和多器官功能衰竭而复杂化,最终死亡。该病例凸显了管理EBV相关ANKL的罕见性和挑战性,强调了早期检测和改进治疗方案的必要性,干细胞移植提供了最佳预后。