• 文献检索
  • 文档翻译
  • 深度研究
  • 学术资讯
  • Suppr Zotero 插件Zotero 插件
  • 邀请有礼
  • 套餐&价格
  • 历史记录
应用&插件
Suppr Zotero 插件Zotero 插件浏览器插件Mac 客户端Windows 客户端微信小程序
定价
高级版会员购买积分包购买API积分包
服务
文献检索文档翻译深度研究API 文档MCP 服务
关于我们
关于 Suppr公司介绍联系我们用户协议隐私条款
关注我们

Suppr 超能文献

核心技术专利:CN118964589B侵权必究
粤ICP备2023148730 号-1Suppr @ 2026

文献检索

告别复杂PubMed语法,用中文像聊天一样搜索,搜遍4000万医学文献。AI智能推荐,让科研检索更轻松。

立即免费搜索

文件翻译

保留排版,准确专业,支持PDF/Word/PPT等文件格式,支持 12+语言互译。

免费翻译文档

深度研究

AI帮你快速写综述,25分钟生成高质量综述,智能提取关键信息,辅助科研写作。

立即免费体验

使用下一代测序鉴定蕈样肉芽肿的致病变体。

Pathogenic variants of mycosis fungoides identified using next-generation sequencing.

作者信息

Shrestha Sunaina, Newsom Kimberly, Chaffin Joanna Melody, Seifert Robert P

机构信息

Department of Pathology, Immunology and Laboratory Medicine, University of Florida College of Medicine, Gainesville, FL, USA.

出版信息

J Hematop. 2024 Dec;17(4):209-214. doi: 10.1007/s12308-024-00607-5. Epub 2024 Sep 19.

DOI:10.1007/s12308-024-00607-5
PMID:39298006
Abstract

Mycosis fungoides (MF), the predominant form of cutaneous T-cell lymphoma (CTCL), poses diagnostic challenges due to its clinical and histological resemblance to benign skin disorders. Delayed diagnosis contributes to therapeutic delays, prompting exploration of advanced diagnostics tools. Next-generation sequencing (NGS) may enhance disease detection by identifying pathogenic variants common to CTCL but absent in benign inflammatory disorders. We aim to discuss novel and common pathogenic variants in CTCL to enhance the utility of NGS as a diagnostic adjunct. This pilot study employed (NGS) to identify pathogenic variants in 10 MF cases. Cases were selected based on PCR-confirmed T-cell receptor clonality, with adequate DNA for NGS. GatorSeq NGS Panel, Illumina NextSeq500, and QIAGEN Clinical Insight QCI software facilitated sequencing, analysis, and variant interpretation. NGS revealed eight novel mutations in genes including HLA-DRB1, AK2, ITPKB, HLA-B, TYRO3, and CHD2. Additionally, previously reported MF-associated mutations such as DNMT3A, STAT5B, and SOCS1 (mouse study only) were detected as well. Detected variants were involved in apoptotic, NF-kB, JAK-STAT, and TCR signaling pathways, providing insights into MF pathogenesis. Mutations in genes like APC, AK2, TYRO3, and ITPKB that regulate tumor proliferation and apoptosis were noted. MF cases were associated with HLA gene mutations. NGS may enhance MF diagnosis, as the detection of pathogenic variants, particularly those known to occur in MF, favors a neoplastic diagnosis over an inflammatory diagnosis. Continuing this work may lead to the discovery of therapeutic targets.

摘要

蕈样肉芽肿(MF)是皮肤T细胞淋巴瘤(CTCL)的主要形式,由于其临床和组织学表现与良性皮肤疾病相似,给诊断带来了挑战。诊断延迟会导致治疗延误,促使人们探索先进的诊断工具。下一代测序(NGS)可能通过识别CTCL中常见但在良性炎症性疾病中不存在的致病变异来提高疾病检测率。我们旨在讨论CTCL中的新型和常见致病变异,以提高NGS作为诊断辅助手段的效用。这项前瞻性研究采用NGS来鉴定10例MF病例中的致病变异。病例是根据PCR确认的T细胞受体克隆性选择的,有足够的DNA用于NGS。GatorSeq NGS Panel、Illumina NextSeq500和QIAGEN Clinical Insight QCI软件有助于测序、分析和变异解读。NGS在包括HLA-DRB1、AK2、ITPKB、HLA-B、TYRO3和CHD2等基因中发现了8个新突变。此外,还检测到了先前报道的与MF相关的突变,如DNMT3A、STAT5B和SOCS1(仅在小鼠研究中)。检测到的变异涉及凋亡、NF-κB、JAK-STAT和TCR信号通路,为MF发病机制提供了见解。注意到调节肿瘤增殖和凋亡的基因如APC、AK2、TYRO3和ITPKB中的突变。MF病例与HLA基因突变有关。NGS可能会提高MF的诊断率,因为致病变异的检测,特别是那些已知在MF中出现的变异,有利于肿瘤性诊断而非炎症性诊断。继续这项工作可能会导致治疗靶点的发现。

相似文献

1
Pathogenic variants of mycosis fungoides identified using next-generation sequencing.使用下一代测序鉴定蕈样肉芽肿的致病变体。
J Hematop. 2024 Dec;17(4):209-214. doi: 10.1007/s12308-024-00607-5. Epub 2024 Sep 19.
2
Mycosis fungoides: differentiation from inflammation and detection of circulating tumour cells with the EuroClonality next-generation sequencing assay.蕈样肉芽肿:通过EuroClonality下一代测序分析与炎症相鉴别及循环肿瘤细胞的检测
Br J Dermatol. 2025 Feb 18;192(3):492-500. doi: 10.1093/bjd/ljae425.
3
T-cell clonality assessment by next-generation sequencing improves detection sensitivity in mycosis fungoides.下一代测序通过 T 细胞克隆性评估提高蕈样肉芽肿的检测灵敏度。
J Am Acad Dermatol. 2015 Aug;73(2):228-36.e2. doi: 10.1016/j.jaad.2015.04.030. Epub 2015 Jun 3.
4
Preliminary assessment of the accuracy of cutaneous T-cell lymphoma diagnosis through deep sequencing of the TRG gene.通过TRG基因深度测序对皮肤T细胞淋巴瘤诊断准确性的初步评估。
Clin Exp Dermatol. 2025 Mar 26;50(4):788-794. doi: 10.1093/ced/llae413.
5
Primary cutaneous T-cell lymphoma (mycosis fungoides and Sézary syndrome): part I. Diagnosis: clinical and histopathologic features and new molecular and biologic markers.原发性皮肤 T 细胞淋巴瘤(蕈样肉芽肿和赛泽里综合征):第一部分。诊断:临床和组织病理学特征以及新的分子和生物学标志物。
J Am Acad Dermatol. 2014 Feb;70(2):205.e1-16; quiz 221-2. doi: 10.1016/j.jaad.2013.07.049.
6
High-throughput sequencing of the T cell receptor β gene identifies aggressive early-stage mycosis fungoides.高通量测序 T 细胞受体 β 基因可鉴定侵袭性早期蕈样肉芽肿。
Sci Transl Med. 2018 May 9;10(440). doi: 10.1126/scitranslmed.aar5894.
7
Whole-genome sequencing reveals oncogenic mutations in mycosis fungoides.全基因组测序揭示蕈样肉芽肿中的致癌突变。
Blood. 2015 Jul 23;126(4):508-19. doi: 10.1182/blood-2014-11-611194. Epub 2015 Jun 16.
8
Genomic analysis reveals recurrent deletion of JAK-STAT signaling inhibitors HNRNPK and SOCS1 in mycosis fungoides.基因组分析显示蕈样肉芽肿中 JAK-STAT 信号通路抑制剂 HNRNPK 和 SOCS1 经常缺失。
Genes Chromosomes Cancer. 2018 Dec;57(12):653-664. doi: 10.1002/gcc.22679. Epub 2018 Oct 25.
9
Molecular staging of lymph nodes from 60 patients with mycosis fungoides and Sézary syndrome: correlation with histopathology and outcome suggests prognostic relevance in mycosis fungoides.60例蕈样肉芽肿和塞扎里综合征患者淋巴结的分子分期:与组织病理学及预后的相关性提示其在蕈样肉芽肿中具有预后意义。
Br J Dermatol. 2006 Oct;155(4):756-62. doi: 10.1111/j.1365-2133.2006.07428.x.
10
Advanced-stage mycosis fungoides: role of the signal transducer and activator of transcription 3, nuclear factor-κB and nuclear factor of activated T cells pathways.晚期蕈样肉芽肿:信号转导和转录激活因子3、核因子κB及活化T细胞核因子通路的作用
Br J Dermatol. 2020 Jan;182(1):147-155. doi: 10.1111/bjd.18098. Epub 2019 Jul 25.

本文引用的文献

1
modelling of cutaneous T-cell lymphoma: The role of SOCS1.皮肤T细胞淋巴瘤的建模:SOCS1的作用
Front Oncol. 2022 Nov 24;12:1031052. doi: 10.3389/fonc.2022.1031052. eCollection 2022.
2
The 5th edition of the World Health Organization Classification of Haematolymphoid Tumours: Lymphoid Neoplasms.《世界卫生组织造血与淋巴组织肿瘤分类》第五版:淋巴肿瘤。
Leukemia. 2022 Jul;36(7):1720-1748. doi: 10.1038/s41375-022-01620-2. Epub 2022 Jun 22.
3
From Benign Inflammatory Dermatosis to Cutaneous Lymphoma. DNA Copy Number Imbalances in Mycosis Fungoides versus Large Plaque Parapsoriasis.
从良性炎症性皮肤病到皮肤淋巴瘤。蕈样肉芽肿与大斑块副银屑病的 DNA 拷贝数失衡。
Medicina (Kaunas). 2021 May 15;57(5):502. doi: 10.3390/medicina57050502.
4
Pembrolizumab in Relapsed and Refractory Mycosis Fungoides and Sézary Syndrome: A Multicenter Phase II Study.派姆单抗治疗复发/难治性蕈样霉菌病和塞扎里综合征:一项多中心 II 期研究。
J Clin Oncol. 2020 Jan 1;38(1):20-28. doi: 10.1200/JCO.19.01056. Epub 2019 Sep 18.
5
The histological prevalence and clinical implications of folliculotropism and syringotropism in mycosis fungoides.蕈样肉芽肿中亲毛囊性和亲汗腺性的组织学患病率及临床意义
Chin Clin Oncol. 2019 Feb;8(1):6. doi: 10.21037/cco.2018.10.02.
6
Chromatin-associated APC regulates gene expression in collaboration with canonical WNT signaling and AP-1.与染色质相关的APC与经典WNT信号通路和AP-1协同调节基因表达。
Oncotarget. 2018 Jul 27;9(58):31214-31230. doi: 10.18632/oncotarget.25781.
7
Molecular advances in cutaneous T-cell lymphoma.皮肤T细胞淋巴瘤的分子进展
Semin Cutan Med Surg. 2018 Mar;37(1):81-86. doi: 10.12788/j.sder.2018.007.
8
Mycosis fungoides-clinical and histopathologic features, differential diagnosis, and treatment.蕈样肉芽肿——临床与组织病理学特征、鉴别诊断及治疗
Semin Cutan Med Surg. 2018 Mar;37(1):2-10. doi: 10.12788/j.sder.2018.002.
9
Standards and Guidelines for the Interpretation and Reporting of Sequence Variants in Cancer: A Joint Consensus Recommendation of the Association for Molecular Pathology, American Society of Clinical Oncology, and College of American Pathologists.癌症序列变异解读与报告的标准和指南:分子病理学协会、美国临床肿瘤学会和美国病理学家学会联合共识推荐
J Mol Diagn. 2017 Jan;19(1):4-23. doi: 10.1016/j.jmoldx.2016.10.002.
10
Genetics of Cutaneous T Cell Lymphoma: From Bench to Bedside.皮肤T细胞淋巴瘤的遗传学:从实验室到临床
Curr Treat Options Oncol. 2016 Jul;17(7):33. doi: 10.1007/s11864-016-0410-8.