Boligo Sofia, Santos Cláudia, Branco Cláudia, Contente Helena
General Surgery Department, Unidade Local de Saúde de Lisboa Ocidental, E.P.E., Estrada Forte do Alto Duque, 1449-995, Lisboa, Portugal.
J Surg Case Rep. 2024 Oct 5;2024(10):rjae624. doi: 10.1093/jscr/rjae624. eCollection 2024 Oct.
Anastomosing hemangioma (AH) is an exceedingly rare benign vascular tumor, often mistaken for malignant neoplasms due to its histological features. First described in 2009, AH has been documented in various sites, including the kidney, liver, and adrenal gland. This report presents a 64-year-old man who, following a bicycle accident, underwent imaging that revealed a nodule suspicious for a paraganglioma in the right para-caval region. Despite the high radiotracer uptake on 68Ga-DOTANOC PET scan, which suggested paraganglioma, the patient remained asymptomatic and laboratory tests ruled out excessive catecholamine secretion. Surgical excision led to a diagnosis of AH, distinguished by its unique anastomosing vascular pattern and histological similarity to angiosarcoma. This case underlines the diagnostic challenges and potential for overtreatment of AH, highlighting the need for heightened awareness and careful histopathological and imaging evaluation to avoid misdiagnosis and ensure appropriate management.
吻合性血管瘤（AH）是一种极其罕见的良性血管肿瘤，由于其组织学特征，常被误诊为恶性肿瘤。AH于2009年首次被描述，已在包括肾脏、肝脏和肾上腺在内的多个部位被记录。本报告介绍了一名64岁男性，在一次自行车事故后接受影像学检查，发现右腔静脉旁区域有一个可疑为副神经节瘤的结节。尽管68Ga-DOTANOC PET扫描显示高放射性示踪剂摄取，提示为副神经节瘤，但患者仍无症状，实验室检查排除了儿茶酚胺分泌过多。手术切除后诊断为AH，其特征为独特的吻合血管模式以及与血管肉瘤的组织学相似性。该病例强调了AH的诊断挑战和过度治疗的可能性，突出了提高认识以及进行仔细的组织病理学和影像学评估以避免误诊并确保适当管理的必要性。
