Ranaivoson Manitra O I, Manassé Herijaona R, Anesy Anselme A C, Lazasoa S D, Bozon Olivier, Daoulas Thomas
Service de Chirurgie Orthopédique du CHU JRA Antananarivo, Madagascar.
Département de Chirurgie Orthopédique, Unité de Chirurgie du Membre Supérieur, de la Main et des Nerfs Périphériques, CHU Lapeyronie, Montpellier, France.
Hand Surg Rehabil. 2025 Apr;44(2):102093. doi: 10.1016/j.hansur.2025.102093. Epub 2025 Jan 22.
We report a case of CAF in the hand of a young adult woman. This patient's age exceeded the usual range for CAF. While surgical excision led to fifth digit stiffness and bowstringing, further diagnostic delays could have resulted in much worse outcomes due to tumor invasion of the tendons. This case suggests reevaluating the upper age limit for diagnosis and considering CAF in adults with suggestive clinical features.
我们报告了一例发生在一名年轻成年女性手部的先天性动静脉瘘(CAF)病例。该患者的年龄超出了CAF的常见范围。虽然手术切除导致了小指僵硬和弓弦状畸形,但由于肿瘤侵犯肌腱,进一步的诊断延迟可能会导致更糟糕的结果。该病例提示应重新评估诊断的年龄上限,并考虑对具有提示性临床特征的成年人进行先天性动静脉瘘的诊断。