Kudo Makoto, Akasaka Manami, Sakuraba Minoru, Murakami Yoichi, Kusano Syuji
Pediatrics, Iwate Medical University Hospital, Shiwa, JPN.
Paediatrics, Iwate Medical University Hospital, Shiwa, JPN.
Cureus. 2025 Feb 26;17(2):e79719. doi: 10.7759/cureus.79719. eCollection 2025 Feb.
Congenital hemangioma (CH) is a rare form of vascular anomaly that develops prenatally, is difficult to differentiate from other vascular anomalies, and poses significant risks, including heart failure and severe hemorrhage. Herein, we present the case of a female infant born with a dark red mass measuring 30 mm × 20 mm in size, located on the right temporal region. She was referred to us for outpatient follow-up but presented to the emergency department on day 21 of life with a massive pulsatile hemorrhage originating from the mass. The patient simultaneously presented with tachycardia and cold extremities. We initiated artificial respiration and compression of the vascular anomalies, and the bleeding was well-controlled. Red blood cell transfusion stabilized her circulation, allowing transfer of the patient to Iwate Medical University Hospital for further evaluation. Owing to difficulties in differentiating CH from other vascular anomalies on imaging, a biopsy was performed. Histological examination revealed a dilated vascular cavity, lined with a single layer of endothelial-like cells with no arterial components. Although hemorrhage from rapidly involutingCH is rare, it is possible that ulceration of the CH could induce hemorrhage.
先天性血管瘤（CH）是一种罕见的血管异常形式，在产前发育，难以与其他血管异常区分开来，并且存在重大风险，包括心力衰竭和严重出血。在此，我们报告一例女婴病例，其出生时右侧颞区有一个大小为30 mm×20 mm的暗红色肿块。她被转诊至我们处进行门诊随访，但在出生后第21天因肿块大量搏动性出血而就诊于急诊科。患者同时出现心动过速和四肢冰冷。我们启动了人工呼吸并对血管异常进行压迫，出血得到了很好的控制。红细胞输注稳定了她的循环，使患者得以转至岩手医科大学医院进行进一步评估。由于在影像学上难以将CH与其他血管异常区分开来，因此进行了活检。组织学检查显示血管腔扩张，内衬单层内皮样细胞，无动脉成分。尽管快速消退型CH出血罕见，但CH溃疡有可能诱发出血。
