Suppr超能文献

退行性和非退行性自闭症患者个体之间表型和基因型差异的比较分析:一项横断面研究。

Comparative Analysis of Phenotypic and Genotypic Differences Between Individuals Affected by Regressive and Non-Regressive Autism: A Cross-Sectional Study.

作者信息

Tonekaboni Seyed Hassan, Iaboni Alana, Trost Brett, Reuter Miriam, Lindenmaier Zsuzsa, Kushki Azadeh, Kelley Elizabeth, Jones Jessica, Ayub Muhammed, Georgiades Stelios, Nicolson Robert, Chan Elim, Cretu Andrada, Brian Jessica, Anagnostou Evdokia

机构信息

Autism Research Centre, Bloorview Research Institute, Holland Bloorview Kids Rehabilitation Hospital, Toronto, Ontario, Canada.

Programs in Molecular Medicine and Genetics and Genome Biology, Hospital for Sick Children, Toronto, Ontario, Canada.

出版信息

Autism Res. 2025 Jun;18(6):1290-1300. doi: 10.1002/aur.70029. Epub 2025 Apr 3.

Abstract

Development among autistic youth varies widely. A subgroup of children experiences regression, defined as the loss of previously acquired developmental skills. Various genetic and environmental factors have been suggested as potential contributors. This study aimed to compare the developmental profiles of children and youth with regression to those without and identify factors associated with regression. Data from the Province of Ontario Neurodevelopmental Disorders (POND) Network was analyzed, including 930 eligible participants. Regression classification was based on the Autism Diagnostic Interview-Revised (ADI-R). Differences in demographic information, medical history, mental health, cognitive and adaptive functioning, and molecular genetic findings were examined between individuals with regressive and non-regressive autism. Among participants, 211 (22.7%) had regressive autism. Lower Full-Scale IQ (p corrected = 0.015) and adaptive function (ABAS-2) scores (p corrected = 0.015) were identified in the regressive group. No statistically significant differences in mental health outcomes (measured by the Child Behavior Checklist, CBCL) or socialization and core symptom severity (measured by the Social Communication Questionnaire, SCQ) were found. There were no notable differences in other factors hypothesized to contribute to regression, such as pregnancy duration, family history of autism, caregivers' education levels, or sleep disorders, except for a higher prevalence of epilepsy in the regressive group (p = 0.001). Rare and common genetic features of both groups are described. In conclusion, autistic youth with regression tend to have lower cognitive and adaptive scores and may experience higher epilepsy rates. Further powered studies are needed to explore the genomic architecture of autistic regression.

摘要

自闭症青少年的发育情况差异很大。有一部分儿童会出现发育倒退,即丧失先前获得的发育技能。多种遗传和环境因素被认为是可能的促成因素。本研究旨在比较有发育倒退和无发育倒退的儿童及青少年的发育概况,并确定与发育倒退相关的因素。对安大略省神经发育障碍(POND)网络的数据进行了分析,包括930名符合条件的参与者。发育倒退分类基于修订版自闭症诊断访谈(ADI-R)。对有发育倒退和无发育倒退的自闭症患者在人口统计学信息、病史、心理健康、认知和适应功能以及分子遗传学发现方面的差异进行了检查。在参与者中,211人(22.7%)患有发育倒退型自闭症。发育倒退组的全量表智商(p校正=0.015)和适应功能(ABAS-2)得分(p校正=0.015)较低。在心理健康结果(通过儿童行为检查表,CBCL测量)或社交及核心症状严重程度(通过社会沟通问卷,SCQ测量)方面未发现统计学上的显著差异。在其他被认为可能导致发育倒退的因素方面,如孕期时长、自闭症家族史、照顾者教育水平或睡眠障碍,除了发育倒退组癫痫患病率较高(p=0.001)外,没有显著差异。描述了两组的罕见和常见遗传特征。总之,有发育倒退的自闭症青少年往往认知和适应得分较低,且可能经历更高的癫痫发病率。需要进一步有足够样本量的研究来探索自闭症发育倒退的基因组结构。

https://cdn.ncbi.nlm.nih.gov/pmc/blobs/190e/12166510/7f31234b467d/AUR-18-1290-g001.jpg

文献AI研究员

20分钟写一篇综述,助力文献阅读效率提升50倍。

立即体验

用中文搜PubMed

大模型驱动的PubMed中文搜索引擎

马上搜索

文档翻译

学术文献翻译模型,支持多种主流文档格式。

立即体验