Yamamura Akitoshi, Taki Mana, Kitamura Sachiko, Sunada Masumi, Yamanoi Koji, Murakami Ryusuke, Shimizu Takayoshi, Yamaguchi Ken, Hamanishi Junzo, Minamiguchi Sachiko, Mandai Masaki
Department of Gynecology and Obstetrics, Kyoto University Graduate School of Medicine, Kyoto, Japan.
Department of Orthopaedic Surgery, Kyoto University Graduate School of Medicine, Kyoto, Japan.
Am J Case Rep. 2025 Apr 3;26:e946680. doi: 10.12659/AJCR.946680.
BACKGROUND Ovarian serous borderline tumors (SBTs) generally have a favorable prognosis, with a very low recurrence rate. However, in rare cases, they can recur as invasive low-grade serous carcinoma (LGSC) after a prolonged follow-up period. Here, we report a case of LGSC originating from SBT that recurred 23 years after the initial surgery, with metastasis to the quadratus lumborum muscle - an exceptionally rare site of metastasis. CASE REPORT A 50-year-old woman, initially diagnosed with stage IIIC SBT and treated with complete tumor resection 23 years prior, presented with an asymptomatic recurrence detected by an elevated serum cancer antigen 125 (CA125) level. Contrast-enhanced computed tomography (CT) revealed multiple nodules suspected of peritoneal dissemination and a tumor infiltrating the quadratus lumborum muscle, suggesting recurrent SBT. A CT-guided needle biopsy confirmed that the tumor within the quadratus lumborum was a recurrence of SBT. Complete cytoreductive surgery was performed with the assistance of an orthopedic surgeon. Histopathological examination revealed progression to LGSC with cytoplasmic expression of the BRAF proto-oncogene (BRAF) V600E, indicating the presence of the BRAF V600E mutation, which is a characteristic feature of both SBT and LGSC. A retrospective review of CT images taken 10 years prior to the recurrence diagnosis showed a peritoneal tumor with calcification attached to the ileocecum, suggesting that the patient had remained asymptomatic for more than a decade after the actual onset of recurrence. CONCLUSIONS This case illustrates a rare instance of recurrent SBT with metastasis to the quadratus lumborum muscle. Given the exceptionally slow progression of recurrent SBT, long-term follow-up with CT imaging and serum CA125 monitoring is crucial for timely intervention and appropriate management upon recurrence.
背景 卵巢浆液性交界性肿瘤(SBTs)通常预后良好,复发率极低。然而,在罕见情况下,经过长时间随访后,它们可能会复发为浸润性低级别浆液性癌(LGSC)。在此,我们报告一例源自SBT的LGSC病例,该病例在初次手术后23年复发,并转移至腰方肌——一个极为罕见的转移部位。
病例报告 一名50岁女性,23年前最初被诊断为IIIC期SBT并接受了肿瘤全切手术,此次因血清癌抗原125(CA125)水平升高而检测出无症状复发。增强计算机断层扫描(CT)显示多个疑似腹膜播散的结节以及一个浸润腰方肌的肿瘤,提示SBT复发。CT引导下针吸活检证实腰方肌内的肿瘤为SBT复发。在一名骨科医生的协助下进行了完整的细胞减灭术。组织病理学检查显示进展为LGSC,伴有BRAF原癌基因(BRAF)V600E的细胞质表达,表明存在BRAF V600E突变,这是SBT和LGSC的特征性表现。对复发诊断前10年拍摄的CT图像进行回顾性分析显示,回盲部附着有钙化的腹膜肿瘤,提示患者在实际复发后十多年一直无症状。
结论 本病例说明了SBT复发并转移至腰方肌的罕见情况。鉴于复发性SBT进展异常缓慢,采用CT成像和血清CA125监测进行长期随访对于复发时的及时干预和恰当管理至关重要。