Tapia Victor S, Withers Sarah E, Zhou Ran, Bennington Abigail, Hoyle Christopher, Hedley Frances, El Khouja Adam, Luka Nadim, Massimo Marco, Crilly Siobhan, Long Katherine R, Lawrence Catherine B, Kasher Paul R
Division of Neuroscience, School of Biological Sciences, Faculty of Biology, Medicine and Health, Manchester Academic Health Science Centre, The University of Manchester, Manchester M13 9PL, UK.
Geoffrey Jefferson Brain Research Centre, The Manchester Academic Health Science Centre, Northern Care Alliance National Health Service (NHS) Foundation Trust, The University of Manchester, Manchester M13 9PL, UK.
Dis Model Mech. 2025 Sep 1;18(9). doi: 10.1242/dmm.052145. Epub 2025 May 23.
The antiviral enzyme cholesterol 25-hydroxylase (CH25H) and its metabolite 25-hydroxycholesterol (25HC), which modulates cholesterol metabolism during infection, have been associated with vascular pathology. Viral infections have been linked to intracerebral haemorrhage (ICH) risk, but the molecular mechanisms leading to ICH via antiviral responses remain unknown. We hypothesised that the CH25H/25HC pathway impacts neuroendothelial integrity in the context of infection-associated ICH. Using a severe acute respiratory syndrome coronavirus 2 (SARS-CoV-2) spike protein-induced zebrafish ICH model and foetal human SARS-CoV-2-associated cortical tissue containing microbleeds, we identified upregulation of CH25H in infection-associated cerebral haemorrhage. Using zebrafish models and human brain endothelial cells, we asked whether 25HC promotes neurovascular dysfunction by modulating cholesterol metabolism. We found that 25HC and pharmacological inhibition of cholesterol synthesis had an additive effect to exacerbate brain bleeding in zebrafish and in vitro neuroendothelial dysfunction. 25HC-induced dysfunction was also rescued by cholesterol supplementation in vitro. These results demonstrate that 25HC can dysregulate brain endothelial function by remodelling cholesterol metabolism. We propose that CH25H/25HC plays an important role in the pathophysiology of brain vessel dysfunction associated with infection and cholesterol dysregulation in the context of ICH.
抗病毒酶胆固醇25 - 羟化酶(CH25H)及其代谢产物25 - 羟胆固醇(25HC)在感染期间调节胆固醇代谢,与血管病变有关。病毒感染与脑出血(ICH)风险相关,但通过抗病毒反应导致ICH的分子机制仍不清楚。我们假设CH25H/25HC途径在感染相关的ICH情况下会影响神经内皮完整性。利用严重急性呼吸综合征冠状病毒2(SARS-CoV-2)刺突蛋白诱导的斑马鱼ICH模型以及含有微出血的胎儿人类SARS-CoV-2相关皮质组织,我们发现在感染相关的脑出血中CH25H上调。利用斑马鱼模型和人脑内皮细胞,我们研究了25HC是否通过调节胆固醇代谢促进神经血管功能障碍。我们发现25HC和胆固醇合成的药理学抑制对斑马鱼脑内出血加剧和体外神经内皮功能障碍具有累加效应。体外补充胆固醇也可挽救25HC诱导的功能障碍。这些结果表明,25HC可通过重塑胆固醇代谢来失调脑内皮功能。我们提出,CH25H/25HC在与感染相关的脑血管功能障碍以及ICH情况下胆固醇失调的病理生理学中起重要作用。