Qin Wei, Lin Sheng-Jia, Zhang Yu, Huang Kevin, Petree Cassidy, Boyd Kevin, Varshney Pratishtha, Varshney Gaurav K
Genes & Human Disease Research Program, Oklahoma Medical Research Foundation, Oklahoma City, Oklahoma, 73104, USA.
Cell & Cancer Biology Research Program, Oklahoma Medical Research Foundation, Oklahoma City, Oklahoma, 73104, USA.
Adv Sci (Weinh). 2025 Jul 20:e09800. doi: 10.1002/advs.202509800.
CRISPR base editors are crucial for precise genome manipulation. Existing APOBEC-based cytosine base editors (CBEs), while powerful, exhibit indels and sequence context limitations, and editing CC and GC motifs is challenging and inefficient. To address these challenges, existing tRNA adenine deaminase (TadA)-derived CBEs are evaluated in zebrafish, and a series of zTadCBE variants is developed that demonstrate high editing efficiency, minimized off-target effects, and an expanded targeting range compared to existing tools. The approach integrates beneficial mutations from TadA-based adenine base editors (ABEs) with SpRYCas9n-enhanced protospacer-adjacent motif (PAM) compatibility. The expanded window zTadCBE variants enable the targeting of cytosines at a broader range of nucleotide positions relative to the PAM sequence, further enhancing the versatility of this tool. Using zTadCBEs, four zebrafish disease models affecting the auditory, nervous, metabolic, and muscular systems are generated directly in the F0 generation-models that cannot be efficiently produced using earlier CBE tools. Together, zTadCBE variants provide a robust and flexible toolkit for efficient and precise C-to-T base editing in zebrafish, facilitating rapid in vivo functional assessment of genetic variants.
CRISPR碱基编辑器对于精确的基因组操作至关重要。现有的基于载脂蛋白B mRNA编辑酶(APOBEC)的胞嘧啶碱基编辑器(CBE)虽然功能强大,但存在插入缺失和序列上下文限制,编辑CC和GC基序具有挑战性且效率低下。为应对这些挑战,研究人员在斑马鱼中评估了现有的源自tRNA腺嘌呤脱氨酶(TadA)的CBE,并开发了一系列zTadCBE变体,与现有工具相比,这些变体表现出高编辑效率、最小化的脱靶效应和扩大的靶向范围。该方法将源自TadA的腺嘌呤碱基编辑器(ABE)的有益突变与SpRYCas9n增强的原间隔相邻基序(PAM)兼容性相结合。扩展窗口zTadCBE变体能够在相对于PAM序列更广泛的核苷酸位置靶向胞嘧啶,进一步增强了该工具的通用性。使用zTadCBE,直接在F0代中生成了四个影响听觉、神经、代谢和肌肉系统的斑马鱼疾病模型,而这些模型使用早期的CBE工具无法有效产生。总之,zTadCBE变体为斑马鱼中高效精确的C到T碱基编辑提供了一个强大而灵活的工具包,有助于对遗传变体进行快速的体内功能评估。