Düzcan Kilimci Duygu, Bal Alkan, Ozkinay Ferda, Ersoy Betül
Departmana of Pediatric Endocrinology, Manisa Celal Bayar University, Faculty of Medicine, Manisa, TUR.
Department of Pediatric Emergency, Manisa Celal Bayar University, Faculty of Medicine, Manisa, TUR.
Cureus. 2025 Jul 1;17(7):e87126. doi: 10.7759/cureus.87126. eCollection 2025 Jul.
The combination of acute pancreatitis (AP), severe hypertriglyceridemia (HTG), and diabetic ketoacidosis (DKA) poses a life-threatening triad. Although DKA is a frequent complication in children, this triad is rare. We report a 10-year-old girl with type 1 diabetes mellitus (T1DM) for 10 months, who presented with DKA, severe HTG, and AP. Her serum was lipemic. She had HTG (1733 mg/dl, 19.5 mmol/L; reference range, 90-129 mg/dl, 1,016-1,456 mmol/L) and severe abdominal pain that did not improve despite treatment for ketoacidosis. She had high lipase levels (1581 U/L, reference range 28-100 U/L), and pancreatitis was detected on abdominal tomography. She recovered with a combination of hydration and insulin therapy. A heterozygous p.N318S (c.953A>G) variant was detected in her lipoprotein lipase (LPL) gene. Her apolipoprotein B (ApoB) was elevated at 1.44 g/L (reference range, 0.6-1.17 g/L, 60-117 mg/dl). It is well established that both the likely pathogenic LPL variants and high ApoB concentrations contribute to an increased risk of cardiovascular complications. Therefore, it is recommended to evaluate for a pathogenic variant in the LPL gene in children with T1DM who do not have dyslipidemia but exhibit the rare triad of AP, HTG, and DKA.
急性胰腺炎(AP)、严重高甘油三酯血症(HTG)和糖尿病酮症酸中毒(DKA)的组合构成了一个危及生命的三联征。虽然DKA在儿童中是一种常见并发症,但这种三联征很罕见。我们报告一名10岁1型糖尿病(T1DM)病程10个月的女孩,她出现了DKA、严重HTG和AP。她的血清呈脂血状。她患有HTG(1733mg/dl,19.5mmol/L;参考范围90 - 129mg/dl,1.016 - 1.456mmol/L),尽管进行了酮症酸中毒治疗,但严重腹痛仍未改善。她的脂肪酶水平很高(1581U/L,参考范围28 - 100U/L),腹部断层扫描检测到胰腺炎。通过补液和胰岛素治疗相结合,她康复了。在她的脂蛋白脂肪酶(LPL)基因中检测到一个杂合的p.N318S(c.953A>G)变异。她的载脂蛋白B(ApoB)升高至1.44g/L(参考范围0.6 - 1.17g/L,60 - 117mg/dl)。众所周知,可能致病的LPL变异和高ApoB浓度都会增加心血管并发症的风险。因此,建议对没有血脂异常但表现出AP、HTG和DKA这一罕见三联征的T1DM儿童评估LPL基因中的致病变异。