Zhu Jun-Yi, Fu Yulong, van de Leemput Joyce, Yu Jing, Li Jinliang, Ray Patricio E, Han Zhe
Center for Precision Disease Modeling, Department of Medicine, University of Maryland School of Medicine, Baltimore, MD 21201, USA.
Division of Endocrinology, Diabetes and Nutrition, Department of Medicine, University of Maryland School of Medicine, Baltimore, MD 21201, USA.
Dis Model Mech. 2025 Jul 1;18(7). doi: 10.1242/dmm.052178. Epub 2025 Aug 1.
People carrying two APOL1 risk alleles (RA) - G1 or G2 - are at greater risk of developing human immunodeficiency virus (HIV)-associated nephropathy (HIVAN). However, it remains unclear whether the encoded protein(s) (APOL1-RA) and HIV-1 Nef interact to induce podocyte cell death. Here, we generated transgenic flies that express APOL1-G1 (derived from a child with HIVAN) and HIV-1 nef specifically in the nephrocytes, the fly equivalent of mammalian podocytes, and assessed their individual and combined effects on the nephrocyte filtration structure and function. We found that HIV-1 Nef acts in synergy with APOL1-G1, resulting in nephrocyte structural and functional defects, and that Nef exacerbates the organelle acidification defects and autophagy reduction induced by APOL1-G1. The synergy between HIV-1 Nef and APOL1-G1 is built on their joint effects on elevating endoplasmic reticulum (ER) stress, triggering nephrocyte dysfunction and, ultimately, cell death. Thus, we identified ER stress as the converging point for the synergy between HIV-1 Nef and APOL1-G1 in inducing nephrocyte cell death. Given the high similarity between Drosophila nephrocytes and human podocytes, our findings suggest ER stress as a new therapeutic target for HIV-1- and APOL1-associated nephropathies.
携带两个载脂蛋白L1(APOL1)风险等位基因(RA)——G1或G2——的人患人类免疫缺陷病毒(HIV)相关性肾病(HIVAN)的风险更高。然而,编码蛋白(APOL1-RA)与HIV-1 Nef是否相互作用以诱导足细胞死亡仍不清楚。在此,我们构建了在肾细胞(果蝇中相当于哺乳动物足细胞)中特异性表达APOL1-G1(源自一名HIVAN患儿)和HIV-1 nef的转基因果蝇,并评估了它们对肾细胞滤过结构和功能的单独及联合影响。我们发现,HIV-1 Nef与APOL1-G1协同作用,导致肾细胞结构和功能缺陷,并且Nef加剧了APOL1-G1诱导的细胞器酸化缺陷和自噬减少。HIV-1 Nef与APOL1-G1之间的协同作用基于它们对升高内质网(ER)应激、引发肾细胞功能障碍并最终导致细胞死亡的联合作用。因此,我们确定ER应激是HIV-1 Nef与APOL1-G1协同诱导肾细胞死亡的汇聚点。鉴于果蝇肾细胞与人类足细胞高度相似,我们的研究结果表明ER应激是HIV-1和APOL1相关肾病的一个新的治疗靶点。